_	EPA/600/R-23/375
£% United States

Environmental Protection	January 2024

m m Agency	www.epa.gov/isa

Integrated Science
Assessment for Lead

Appendix 7: Hematological Effects

January 2024

Center for Public Health and Environmental Assessment
Office of Research and Development
U.S. Enviromnental Protection Agency


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DISCLAIMER

This document has been reviewed in accordance with the U.S. Environmental Protection Agency
policy and approved for publication. Mention of trade names or commercial products does not constitute
endorsement or recommendation for use.

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DOCUMENT GUIDE

This Document Guide is intended to orient readers to the organization of the Lead (Pb) Integrated
Science Assessment (ISA) in its entirety and to the sub-section of the ISA at hand (indicated in bold). The
ISA consists of the Front Matter (list of authors, contributors, reviewers, and acronyms), Executive
Summary, Integrated Synthesis, and 12 appendices, which can all be found at
https://asscssmcnts.cpa.go\/isa/documcnt/&dcid=359536.

Front Matter

Executive Summary

Integrated Synthesis

Appendix 1. Lead Source to Concentration

Appendix 2. Exposure, Toxicokinetics, and Biomarkers

Appendix 3. Nervous System Effects

Appendix 4. Cardiovascular Effects

Appendix 5. Renal Effects

Appendix 6. Immune System Effects

Appendix 7. Hematological Effects

Appendix 8. Reproductive and Developmental Effects

Appendix 9. Effects on Other Organ Systems and Mortality

Appendix 10. Cancer

Appendix 11. Effects of Lead in Terrestrial and Aquatic Ecosystems
Appendix 12. Process for Developing the Pb Integrated Science Assessment

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CONTENTS

DOCUMENT GUIDE 	7-iii

LIST OF TABLES 	7-v

LIST OF FIGURES 	7-vi

ACRONYMS AND ABBREVIATIONS	7-vii

APPENDIX 7 HEMATOLOGICAL EFFECTS	7-1

7.1	Introduction, Summary of the 2013 Integrated Science Assessment for Lead, and Scope

of the Current Review	7-1

7.1.1.	Red Blood Cell Survival and Function	7-2

7.1.2.	Heme Synthesis	7-2

7.2	Scope	7-3

7.3	Red Blood Cell Survival and Function	7-5

7.3.1.	Epidemiologic Studies of Red Blood Cell Survival and Function	7-5

7.3.2.	Toxicological Studies of Red Blood Cell Survival and Function	7-7

7.3.3.	Integrated Summary of Red Blood Cell Survival and Function	7-9

7.4	Heme Synthesis	7-10

7.4.1.	Epidemiologic Studies of Heme Synthesis	7-10

7.4.2.	Toxicological Studies of Heme Synthesis	7-10

7.4.3.	Integrated Summary of Heme Synthesis	7-11

7.5	Biological Plausibility	7-11

7.5.1.	Decreased Red Blood Cell Survival and Function	7-14

7.5.2.	Altered Heme Synthesis	7-15

7.6	Summary and Causality Determination	7-17

7.6.1.	Causality Determination for Red Blood Cell Survival and Function	7-17

7.6.2.	Evidence for Red Blood Cell Survival and Function	7-17

7.6.3.	Evidence for Heme Synthesis	7-18

7.6.4.	Causality Determination	7-19

7.7	Evidence Inventories—Data Tables to Summarize Study Details	7-25

7.8	References	7-32

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LIST OF TABLES

Table 7-1	Summary of evidence indicating a causal relationship between Pb exposure and

hematological effects	7-20

Table 7-2	Epidemiologic studies of exposure to Pb and hematological effects 	7-25

Table 7-3	Animal toxicological studies of Pb exposure and hematological effects	7-30

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LIST OF FIGURES

Figure 7-1	Potential biological plausibility pathways for hematological effects associated with

exposure to Pb. 	7-13

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ACRONYMS AND ABBREVIATIONS

ALAD	S-aminolevulinic acid dehydratase

ALA	aminolevulinic acid

AQCD	Air Quality Criteria Document

BLL	blood lead level

BMI	body mass index

BW	body weight

Ca2+	calcium ion(s)

CAT	catalase

CI	confidence interval

e-waste	electronic waste

EPO	erythropoietin

Fe2+	iron ion

GFAAS	graphite furnace atomic absorption

spectrometry

GPx	glutathione peroxidase

GR	glutathione reductase

GSH	glutathione

GSSG	glutathione disulfide

Hb	hemoglobin

Hct	hematocrit

HSC	hematopoietic stem cell

hr	hour(s)

H2O2	hydrogen peroxide

ICP-MS	inductively coupled plasma mass
spectrometry

ISA	Integrated Science Assessment

KNHANES	Korea National Health and Nutrition

Examination Survey

In	natural log

M	male

M/F	male/female

MCH	mean corpuscular hemoglobin

MCHC	mean corpuscular hemoglobin

concentration

MC V	mean corpuscular volume

MDA	malondialdehyde

Mg2+	magnesium ion

mo	month(s)

OH	hydroxyl radical

NCE	normochromatic erythrocytes

NR	not reported

O2-	superoxide

OR	odds ratio

Pb	lead

PCE	polychromatic erythrocytes

PCV	packed cell volume

PECOS	Population, Exposure, Comparison,
Outcome, and Study Design

Pit	platelet

PND	postnatal day

PS	phosphatidylserine

Q	quartile

RBC	red blood cell

RDW	red blood cell distribution width

ROS	reactive oxygen species

SD	standard deviation

SES	socioeconomic status

SOD	superoxide dismutase

U.S. EPA	United States Environmental Protection
Agency

wk	week(s)

yr	year(s)

Zn	zinc

ZPP	zinc-protoporphyrin

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APPENDIX 7

HEMATOLOGICAL EFFECTS

Causality Determination for Pb Exposure and Hematological Effects

This appendix characterizes the scientific evidence that supports the causality
determination for lead (Pb) exposure and hematological effects. The types of studies
evaluated within this appendix are consistent with the overall scope of the ISA as
detailed in the Process Appendix (see Section 12.4). In assessing the overall evidence,
the strengths and limitations of individual studies were evaluated based on scientific
considerations detailed in Table 12-5 of the Process Appendix (Section 12.6.1). More
details on the causal framework used to reach these conclusions are included in the
Preamble to the ISA (U.S. EPA. 2015). The evidence presented throughout this
appendix supports the following causality determination:

Outcome	Causality Determination

Hematological Effects, Including Altered
Heme Synthesis and Decreased Red	Causal

Blood Cell Survival and Function

The Executive Summary, Integrated Synthesis, and all other appendices of this Pb
ISA can be found at https://assessments.epa.gov/isa/document/&deid=359536.

7.1 Introduction, Summary of the 2013 Integrated Science
Assessment for Lead, and Scope of the Current Review

Hematology is a subgroup of clinical pathology concerned with the morphology, physiology, and
pathology of blood and blood-forming tissues. Hematological measures, when evaluated with information
on other biomarkers, are informative diagnostic tests for blood-forming tissues (i.e., bone marrow, spleen,
and liver) and organ function.

The 2013 Integrated Science Assessment for Lead (hereinafter referred to as the 2013 Pb ISA)
issued causality determinations for hematological effects resulting from lead (Pb) exposure on red blood
cell (RBC) survival and function and altered heme synthesis (U.S. EPA. 2013). The evidence
underpinning these causality determinations is summarized below. Given the interconnectedness of the
effects of Pb on RBC survival and function and altered heme synthesis, this assessment presents a single
causality determination for Pb exposure and hematological effects. This approach allows for a more
holistic evaluation of inter-related health endpoints, including a discussion of how all individual lines of
evidence contribute to the overall hematological effects causality determination.

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7.1.1.

Red Blood Cell Survival and Function

The body of epidemiologic and toxicological evidence assessed in the 2013 Pb ISA indicates a
"causal" relationship between Pb exposure and decreased RBC survival and function. Experimental
animal studies demonstrate that relevant human blood Pb levels (BLLs) from oral and inhalation exposure
alter several hematological parameters (e.g., RBC number), increase measures of oxidative stress
(e.g., inhibition of antioxidant enzymes in RBCs), and increase cytotoxicity in RBC precursor cells. Some
of these effects have been observed in animal toxicological studies with exposures resulting in BLLs of
2-7 (ig/dL. Evidence of biologically plausible modes of action, including increased intracellular calcium

2+

concentrations [Ca ] decreased Ca2+/Mg2+ ATPase activity, and increased phosphatidylserine (PS)

exposure leading to RBC destruction by macrophages, support these findings. Epidemiologic studies
reported associations between exposure to Pb, BLL, and altered hematological endpoints, increased
measures of oxidative stress, and altered hematopoiesis in adults and children. Although most of these
studies are limited by their lack of rigorous methodology (i.e., correlations, t tests, or chi squared
analyses), some studies in children did adjust for potential confounding factors, including age, sex,
mouthing behavior, anemia, dairy product consumption, maternal age, education, employment, marital
status, family structure, and socioeconomic status (SES)-related variables. Though limited in number,
studies that adjusted for confounders also reported consistent associations between BLL and altered
hematological parameters, strengthening their support for findings in experimental animals. Collectively,
the strong evidence from toxicological studies supported by findings from mode of action and
epidemiologic studies reviewed in the 2013 Pb ISA was sufficient to conclude that there is a causal
relationship between Pb exposures and decreased RBC survival and function.

7.1.2. Heme Synthesis

Available toxicological evidence evaluated in the 2013 Pb ISA indicated a causal relationship
between Pb exposure and altered heme synthesis (U.S. EPA. 2013). Altered heme synthesis is
demonstrated by a small but consistent body of studies in adult animals, which report that exposures that
result in BLLs relevant to humans (e.g., 10 (ig/dL) lead to decreased S-aminolevulinic acid dehydratase
(ALAD) and ferrochelatase activities. Supporting this evidence is a larger body of ecotoxicological
studies that demonstrate decreased ALAD activity across a wide range of taxa exposed to Pb. Evidence of
biologically plausible modes of action, including evidence that Pb acts directly on two enzymes involved
in heme synthesis (ALAD and ferrochelatase), decreased RBC Hb concentration, measures of oxidative
stress, and evidence that administration of antioxidants reduced the effects of Pb exposure on antioxidant
enzymes, support these findings. Epidemiologic studies find associations in both adults and children
between higher BLLs and decreased ALAD and ferrochelatase activities. Although most of these studies
are limited by their lack of rigorous methodology and consideration of potential confounders, some
studies in children did incorporate potential confounding factors (i.e., age, sex, urban/rural residence,

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height, weight, body mass index [BMI]). Although limited in number, studies that adjusted for
confounders also reported consistent associations between BLLs and decreased ALAD and ferrochelatase,
strengthening support for the findings in the animal toxicological studies. Evidence for altered heme
synthesis is also provided by a large body of toxicological and epidemiologic studies that report decreased
hemoglobin (Hb) concentrations in association with Pb exposure or BLL. The 2013 Pb ISA concluded
that, collectively, the strong evidence from toxicological and ecotoxicological studies—supported by
findings from epidemiologic studies—is sufficient to conclude a causal relationship between Pb
exposures and altered heme synthesis.

This ISA determined causality for adverse effects of Pb exposure on altered heme Synthesis and
decreased RBC survival and function. Recent evidence demonstrates that Pb exposures alter several
hematological parameters, decrease enzyme activity related to heme synthesis, and increase RBC
oxidative stress. Biological plausibility is provided by toxicological and epidemiologic studies
demonstrating increased intracellular calcium concentrations, decreased Ca2+/Mg2+ ATPase activity, and
increased PS exposure. Taken together, there is sufficient evidence to conclude that there is a causal
relationship between Pb exposure and hematological effects, including altered heme synthesis and
decreased RBC survival and function.

The following sections provide an overview of the scope of the appendix (Section 7.2), evaluation
of the scientific evidence relating Pb exposures and hematological effects (Sections 7.3 and 7.4), a
discussion of biological plausibility (Section 7.5), and a summary section with the updated causality
determination (Section 7.6, Table 7-1). The focus of these sections is on studies published since the
completion of the 2013 Pb ISA (U.S. EPA. 2013). Study-specific details, including animal type, exposure
concentrations and exposure durations in experimental studies, and study design; exposure metrics; and
select results in epidemiologic studies are presented in evidence inventories in Section 7.7.

7.2 Scope

The scope of this section is defined by Population, Exposure, Comparison, Outcome, and Study
Design (PECOS) statements. The PECOS statement defines the objectives of the review and establishes
study inclusion criteria, thereby facilitating identification of the most relevant literature to inform the Pb
ISA.1 To identify the most relevant literature, the body of evidence from the 2013 Pb ISA was considered
in the development of the PECOS statements for this appendix. Specifically, well-established areas of
research; gaps in the literature; and inherent uncertainties in specific populations, exposure metrics,

'The following types of publications are generally considered to fall outside the scope and are not included in the
ISA: review articles (which typically present summaries or interpretations of existing studies rather than bringing
forward new information in the form of original research or new analyses), Pb poisoning studies or clinical reports
(e.g., involving accidental exposures to very high amounts of Pb described in clinical reports that may be extremely
unlikely to be experienced under ambient air exposure conditions), and risk or benefits analyses (e.g., that apply
concentration-response functions or effect estimates to exposure estimates for differing cases).

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comparison groups, and study designs identified in the 2013 Pb ISA inform the scope of this appendix.
The 2013 Pb ISA used different inclusion criteria than the current ISA, and the studies referenced therein
often do not meet the current PECOS criteria (e.g., due to higher or unreported biomarker levels). Studies
that were included in the 2013 Pb ISA, including many that do not meet the current PECOS criteria, are
discussed in this appendix to establish the state of the evidence prior to this assessment. With the
exception of supporting evidence used to demonstrate the biological plausibility of Pb-associated
hematological effects, recent studies were only included if they satisfied all of the components of the
following discipline-specific PECOS statements:

Epidemiologic Studies

Population: Any human population, including specific populations or lifestages that might be at
increased risk of a health effect;

Exposure: Exposure to Pb2 as indicated by biological measurements of Pb in the body, with a
specific focus on Pb in blood, bone, and teeth; validated environmental indicators of Pb
exposure3; or intervention groups in randomized trials and quasi-experimental studies;

Comparison: Populations, population subgroups, or individuals with relatively higher versus
lower levels of the exposure metric (e.g., per unit or log unit increase in the exposure metric,
or categorical comparisons between different exposure metric quantiles);

Outcome: Hematological effects including but not limited to disruption of heme synthesis and
RBC survival and function; and

Study Design: Epidemiologic studies consisting of longitudinal and retrospective cohort studies,
case-control studies, cross-sectional studies with appropriate timing of exposure for the health
endpoint of interest, randomized trials, and quasi-experimental studies examining
interventions to reduce exposures.

Experimental Studies

Population: Laboratory nonhuman mammalian animal species (e.g., mouse, rat, guinea pig,
minipig, rabbit, cat, dog) of any lifestage (including preconception, in utero, lactation,
peripubertal, and adult stages);

2Recent studies of occupational exposure to Pb were only considered insofar as they addressed a topic area that was
relevant to the National Ambient Air Quality Standards review (e.g., longitudinal studies designed to examine recent
versus historical Pb exposure).

3Studies that estimate Pb exposure by measuring Pb concentrations in particulate matter with a nominal mean
aerodynamic diameter less than or equal to 10 |im3 (PMio) and particulate matter with a nominal mean aerodynamic
diameter less than or equal to 2.5 |im3 (PM2 5) ambient air samples are only considered for inclusion if they also
include a relevant biomarker of exposure. Given that size distribution data for Pb-PM are limited, it is difficult to
assess the representativeness of these concentrations to population exposure [Section 2.5.3 (U.S. EPA. 2013)1.
Moreover, data illustrating the relationships of Pb-PMio and Pb-PNfc.s with BLLs are lacking.

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Exposure: Oral, inhalation or intravenous treatment(s) administered to a whole animal (in

vivo) that results in a BLL of 30 pg/dL or below;4'5
Comparators: A concurrent control group exposed to vehicle-only treatment or untreated
control;

Outcome: Hematological effects; and

Study design: Controlled exposure studies of animals in vivo.

7.3 Red Blood Cell Survival and Function

Toxicological and epidemiologic studies evaluated in the 2013 Pb ISA (U.S. EPA, 2013)
provided strong evidence that exposure to Pb affects a range of hematological outcomes related to RBC
survival and function; which is consistent with epidemiologic evidence from the 2006 Pb Air Quality
Criteria Document (AQCD) (U.S. EPA, 2006), demonstrating an association between high BLLs and
anemia in children. Given the extensive evidence base at higher BLLs, the scope for this appendix focuses
on toxicological studies conducted at lower exposure levels and epidemiologic studies in nonoccupational
populations (as described in Section 7.2). Under the defined PECOS criteria, recent toxicological and
epidemiologic studies provide additional support for Pb-related changes in Hb concentration and some
other hematological measures of RBC survival and function. Below, recent evidence is reviewed in the
context of evidence from past assessments.

7.3.1. Epidemiologic Studies of Red Blood Cell Survival and Function

The epidemiologic evidence evaluated in the 2013 Pb ISA (U.S. EPA. 2013) covered a range of
measures related to RBC survival and function, including RBC counts and other hematological
parameters, hematopoiesis, Ca2+/Mg2+ ATPase activity, PS exposure, and RBC oxidative stress.
Specifically, epidemiologic studies provided evidence that elevated BLLs in children and adults are
associated with altered hematological parameters (e.g., decreased RBC counts, Hb concentration, and
hematocrit [Hct] and changes in mean corpuscular volume [MCV] and mean corpuscular hemoglobin
[MCH]), increased measures of oxidative stress (e.g., altered antioxidant enzyme activities [superoxide
dismutase (SOD), catalase (CAT), glutathione peroxidase (GPx)], decreased cellular glutathione (GSH),
and increased lipid peroxidation), and altered hematopoiesis (e.g., decreased erythropoietin [EPO]).
Notably, most of these epidemiologic studies are cross-sectional in design and conducted either in

4Pb mixture studies are included if they employ an experimental arm that involves exposure to Pb alone.

5This level is approximately an order of magnitude above the upper end of the distribution of U.S. young children's
BLLs. The 95th percentile of the 2011-2016 National Health and Nutrition Examination Survey distribution of BLL
in children (1-5 years; n = 2,321) is 2.66 (ig/dL dL (CDC. 2019) and the proportion of individuals with BLL that
exceed this concentration varies depending on factors including (but not limited to) housing age, geographic region,
and a child's age, sex and nutritional status.

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occupationally exposed populations or other populations with higher mean Pb exposures (i.e., BLLs
>10 (ig/dL). These studies were additionally limited by their lack of consideration of potential
confounders, although some studies in children did adjust for a range of factors, including age, sex,
mouthing behavior, anemia, dairy product consumption, maternal age, education, employment, marital
status, family structure, and SES-related variables (Oucirolo et al.. 2010; Ahamed et al.. 2007; Riddell et
al.. 2007). Studies that did account for potential confounders reported consistent associations between
higher BLLs and lower Hb levels, higher prevalence of anemia, and higher levels of RBC oxidative stress
(Sections 4.7.2.1 and 4.7.2.7 of the 2013 Pb ISA). As a whole, the cross-sectional study designs, higher
exposures, and lack of rigorous statistical methodologies in many studies raise uncertainties in the
epidemiologic evidence regarding the directionality of effects; the level, timing, frequency, and duration
of Pb exposure that contributed to the observed associations; and whether the observed associations are
independent of potential confounders.

Recent epidemiologic studies provide generally consistent evidence of inverse associations
between Pb exposures and Hb levels in children. These associations are reported at lower BLLs than in
studies included in the 2013 Pb ISA. Evidence for associations with other hematological parameters of
RBC function and survival, as well as Hb levels in adults, is less robust. Consistent with the 2013 Pb ISA,
most recent studies are cross-sectional analyses, which are unable to establish temporality between
exposure and outcome. Recent studies include populations with lower mean BLLs and more robust
adjustment for potential confounders compared with studies included in the 2013 Pb ISA. Measures of
central tendency for BLLs used in each study, along with other study-specific details including study
population characteristics and select effect estimates, are highlighted in Table 7-2. An overview of the
recent evidence is provided below.

The most common hematological parameter evaluated in recent epidemiologic studies is Hb
levels. A number of cross-sectional studies of children in China observed lower Hb levels associated with
higher blood Pb or erythrocyte Pb levels (Guo et al.. 2021; Kuang et al.. 2020; Li et al.. 2018; Liu et al..
2015; Liu et al.. 2012). Kuang et al. (2020) and Li et al. (2018) also reported inverse associations between
BLLs and MCH in children, which is a measure of average Hb concentration in a single erythrocyte.
Notably, all of these studies had mean and/or median BLLs below 10 (ig/dL, including some below
5 (ig/dL (Guo et al.. 2021; Kuang et al.. 2020; Liu et al.. 2012). While only a few studies attempted to
account for potential confounding by SES (Kuang et al.. 2020; Liu et al.. 2015). others adjusted directly
for iron deficiency (Li et al.. 2018; Liu et al.. 2012). which may be the direct mechanism by which SES
could potentially confound the relationship between BLLs and Hb (i.e., via nutritional deficiency).
Although the magnitude of the observed effect estimates was not directly comparable across studies,
BLLs were negatively associated with Hb levels in all studies. Notably, Liu et al. (2012) reported that
each 1 (ig/dL higher BLL was associated with a larger decrement in Hb levels when restricting their
sample to children with BLLs less than 10 (ig/dL (-0.174 g/dL [95% confidence interval (CI): -0.27,
-0.078 g/dL]) compared with the full sample (-0.096 g/dL [95% CI: -0.18, -0.012 g/dL]). In studies that
examined quantiles of exposure, blood or erythrocyte Pb levels were only associated with Hb levels at the

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higher quantiles (Guo et al.. 2021; Liu et al.. 2015). For example, in a large hospital-based study in China,
children with BLLs between 3.33 and 4.50 (ig/dL (quintile 4) and those with levels greater than
4.50 (ig/dL (quintile 5) had lower Hb levels relative to children with BLLs less than 1.61 (ig/dL
(-0.49 g/L [95% CI: -0.94, -0.04 g/L] and -1.25 g/L [95% CI: -1.71, -0.78 g/L], respectively);
however, null associations were reported for quintiles 2 (1.61-2.44 (ig/dL) and 3 (2.44-3.33 (ig/dL)
relative to the lowest quintile of exposure (Guo et al.. 2021). While the clinical relevance of small mean
decrements in Hb across exposure quintiles is unclear, Guo et al. (2021) also reported that the odds of
anemia (defined as Hb levels below 110 g/L) were monotonically higher in association with higher blood
Pb quintiles, with 45% (95% CI: 26%, 67%) higher odds of anemia for children in the highest quintile of
exposure relative to the lowest quintile. Similarly, Li et al. (2018) observed 5% (95% CI: 0%, 11%)
higher odds of low Hb levels (<115 g/L) per 1 (ig/dL higher BLL.

Recent studies of Pb exposure and Hb levels in adults are more limited in number and include
overlapping study populations. In contrast to studies in children, Park and Lee (2013) reported higher Hb
associated with higher BLLs for adult participants of the 2008—2010 cycles of the Korea National Health
and Nutrition Examination Survey (KNHANES). The analysis was stratified to examine effect
modification by sex and the observed associations were comparable for men and women. A similar study
analyzed the same KNHANES cycles, but examined the population as a whole, rather than stratified by
sex, and also categorized exposure into quartiles (Kim and Lee. 2013). The authors noted similar positive
associations between blood Pb and Hb levels. However, Kim and Lee (2013) observed inverse
associations across exposure quartiles when correcting BLLs for Hct in order to estimate erythrocyte Pb.
As described in the 2006 Pb AQCD (U.S. EPA. 2006). Pb exposure decreases Hct and MCV, meaning
the negative effects of Pb can potentially decrease Pb levels in whole blood.

In addition to studies examining the relationship between Pb exposure and Hb levels, a few recent
cross-sectional studies evaluate associations between BLLs and other hematological parameters. In a
group of children in China, including some living near a battery plant or a lead/-zinc mine, Li et al. (2018)
reported higher odds of low RBC counts and low blood platelets (Pits) in association with higher BLLs.
In contrast, Kuang et al. (2020) observed a positive association with increased RBC counts in a
convenience sample of slightly older boys in Nanjing, China, with notably lower median BLLs
(2.61 (ig/dL compared with 8.38 (ig/dL). In an adult population, a cohort of pregnant women in Durango,
Mexico, La-Llave-Leon et al. (2015) also observed a positive cross-sectional association between RBC
counts and BLLs. Given this small body of studies that examine diverse populations with varying BLLs,
it is difficult to discern methodological or demographic factors contributing to the inconsistent results.

7.3.2. Toxicological Studies of Red Blood Cell Survival and Function

As previously reported in the 2013 Pb ISA, epidemiologic evidence is coherent with experimental
animal studies demonstrating that exposures via drinking water and oral gavage resulting in BLLs

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relevant to what was found in humans affect multiple hematological outcomes related to RBC survival
and function (U.S. EPA. 2013). Specifically, exposure to Pb has been shown to decrease RBC survival,
either through direct effects on RBC membranes leading to increased fragility or through the induction of
eryptosis and eventual phagocytosis by macrophages (U.S. EPA. 2013). Some of these effects have been
observed in animal toxicological studies with exposures resulting in 2-7 (ig/dL BLL. For example, Hb
concentrations in plasma significantly decreased in male mice exposed to Pb nitrate (50 mg/kg BW in
drinking water for 40 days; BLL: 1.72 ± 0.02 (ig/dL) (Sharma et al.. 2010). BLLs >100 (ig/dL were also
associated with decreased RBC survival in laboratory animals.

The evidence is limited and conflicting for the observed effects of Pb exposure on hematopoiesis
in rats and mice. For example, administration of Pb acetate (140, 250, or 500 mg/kg) via oral gavage once
per week for 10 weeks decreased the number of polychromatic RBCs (PCE) and increased numbers of
micronucleated PCEs in female rats (Celik et al.. 2005). Increased micronucleated PCEs were reported in
female and male rats exposed to Pb acetate in drinking water for 125 days, but decreased
PCEs/normochromatic RBCs (NCEs) ratio was only observed in male rats (Alghazal et al.. 2008).
However, in mice exposed to Pb acetate (1 g/L in drinking water for 90 days), PCE increased, but
PCE/NCE was unaffected (Marques et al.. 2006).

In addition, the 2013 Pb ISA reported that Pb exposure significantly decreases several
hematological parameters. In studies reporting BLL relevant to this ISA, decreased RBC counts
(Andielkovic et al.. 2019; Cai et al.. 2018; Sharma et al.. 2010). Hb concentration (Andielkovic et al..
2019; Cai et al.. 2018; Berrahal et al.. 2011; Sharma et al.. 2010; Baranowska-Bosiacka et al.. 2009;
Masso-Gonzalez and Antonio-Garcia. 2009). and Hct (Andielkovic et al.. 2019; Masso-Gonzalez and
Antonio-Garcia. 2009; Masso et al.. 2007) were reported in laboratory studies conducted in rats. In other
studies in which BLLs were not reported, decreased RBC counts (Simsek et al.. 2009; Marques et al..
2006; Lee et al.. 2005). Hb (Wang et al.. 2010b; Simsek et al.. 2009; Lee et al.. 2005). Hct (Molina et al..
2011; Marques et al.. 2006; Lee et al.. 2005). MCV (Wang et al.. 2010b). MCH (Wang et al.. 2010b;
Simsek et al.. 2009). and mean corpuscular hemoglobin concentration (MCHC) (Wang et al.. 2010b;
Simsek et al.. 2009) were reported in laboratory studies conducted in rats and mice. Some toxicological
studies found no evidence of hematological effects (Gautam and Flora. 2010; Lee et al.. 2006).

Recent studies also report effects of Pb exposure on hematological parameters at BLLs relevant to
this ISA. Administration of Pb acetate in drinking water (0.2%; BLL = 9.3 ± 0.98 (ig/dL) for 84 days
resulted in RBC hemolysis, and significantly decreased RBC lifespan and number, and Hb levels, but had
no effect on Pit number in blood collected from Sprague Dawley rats (Cai et al.. 2018). In a different
study, administration of Pb acetate in drinking water (0.150 mg/kg; BLL = 14.7 (ig/dL) for 1 day
decreased RBCs, Pits, Hb concentration, and Hct, but had no effect on MCV, MCH an MCHC in whole
blood collected from adult male Wistar rats (Andielkovic et al.. 2019). Pb acetate treatment increased Hct
and RBC distribution width, decreased MCHC, and had no effect on RBC number, Hb, MCV, and MCH
in adult male C57BJ mice exposed via drinking water (200 ppm; BLL = 21.6 (ig/dL) for 45 days (Corsetti

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et al.. 2017). The potential effects of Pb exposure in rats were also investigated through a combination of
lactational and drinking water exposures. Beginning on postnatal day (PND) 1, dams were given drinking
water containing Pb acetate (50 mg/L). On PND 21, male pups were subsequently administered Pb
acetate (50 mg/L) in drinking water for an additional 40 or 65 days, at which time they were sacrificed.
Hct was significantly reduced in mice exposed until PND 40 (BLL = 12.67 ± 1.68 (ig/dL) whereas Hct
and Hb were significantly decreased at PND 65 (BLL = 7.49 ± 0.78 (ig/dL) (Berrahal et al.. 2011). Study-
specific details, including animal species, strain, sex, and BLLs are highlighted in Table 7-3.

7.3.3. Integrated Summary of Red Blood Cell Survival and Function

Experimental animal studies evaluated in the 2013 Pb ISA (U.S. EPA. 2013) demonstrate that Pb
exposures resulting in BLLs relevant to humans (i.e., <10 (ig/dL) alter several hematological parameters,
increase measures of oxidative stress, and increase cytotoxicity in RBC precursor cells. While
epidemiologic evidence synthesized in the last review was generally coherent with results from the animal
studies, most of the epidemiologic studies evaluated are cross-sectional, were conducted in populations
with higher mean Pb exposures (i.e., BLLs >10 (.ig/dL). did not thoroughly consider potential
confounders, and lacked rigorous statistical methodology. As a result, there were considerable
uncertainties in the epidemiologic evidence regarding the directionality of effects; the level, timing,
frequency, and duration of Pb exposure that contributed to the observed associations; and whether the
observed associations are independent of potential confounders.

Though limited in number, recent PECOS-relevant animal toxicological studies continue to
support the findings from the last review. Specifically, these studies consistently report the effects of Pb
on hematological parameters, including mostly consistent evidence of a Pb-related decrease in Hb. Recent
epidemiologic studies expand on the evidence presented in the 2013 Pb ISA and provide additional
support for the experimental evidence. Although the recent studies are also cross-sectional, they include
populations with much lower BLL means (<10 (ig/dL) and include more robust adjustment for potential
confounding, addressing important uncertainties from the last review. The most consistent epidemiologic
evidence indicates an association between BLLs and decreased Hb levels in children, which is coherent
with the evidence from recent experimental animal studies. While the clinical relevance of small mean
decrements in Hb is unclear, a few of the recent epidemiologic studies include analyses linking increased
BLLs to increased prevalence of anemia. Recent epidemiologic studies of Hb levels in adults were more
limited in number and less consistent than those in children. Additionally, of the relatively few studies
examining RBC counts, the results were also inconsistent.

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7.4 Heme Synthesis

Toxicological and ecotoxicological studies evaluated in the 2006 Pb AQCD (U.S. EPA, 2006)
and the 2013 Pb ISA (U.S. EPA. 2013) provided strong evidence that exposure to Pb affects heme
synthesis. A limited number of epidemiologic studies contributed compelling supporting evidence. Given
the extensive evidence base at higher BLLs, the scope for this appendix focuses on toxicological studies
conducted at lower exposure levels and epidemiologic studies in nonoccupational populations (as
described in Section 7.2). Below, recent evidence is reviewed in the context of evidence from past
assessments.

7.4.1. Epidemiologic Studies of Heme Synthesis

The epidemiologic studies evaluated in the 2013 Pb ISA (U.S. EPA. 2013) provided evidence that
BLLs in children and adults are associated with decreased activity of enzymes involved in the heme
synthesis pathway, including ALAD and ferrochelatase. Similar to studies of RBC function and survival,
most studies on heme synthesis are cross-sectional in design and conducted either in occupationally
exposed populations and/or in populations with higher mean Pb exposures (i.e., BLL >20 (ig/dL). These
studies were additionally limited by their lack of consideration of potential confounders, although some
studies adjusted for or considered potential confounding factors (i.e., age, sex, urban/rural residence,
height, weight, and BMI) (Wang et al.. 2010a; Ahamed et al.. 2007; Ahamed et al.. 2006). Studies that did
account for potential confounders reported consistent inverse associations between BLLs and ALAD
activity (Section 4.7.3.1 of the 2013 Pb ISA). Evidence for altered heme synthesis is also provided by the
epidemiologic studies discussed in Section 7.3.1 that report lower Hb concentrations in association with
higher Pb exposure or BLLs. Decreased RBC survival and hematopoiesis can be expected to occur
simultaneously, and any effect on Hb levels is likely a combination of the two processes. Outside of the
recent studies on Hb concentrations discussed in Section 7.3.1, there are no recent PECOS-relevant
epidemiologic studies examining the relationship between Pb exposure and heme synthesis.

7.4.2. Toxicological Studies of Heme Synthesis

Pb-induced alterations in heme synthesis occurring at BLLs relevant to this ISA (e.g., 10 (ig/dL)
have been demonstrated convincingly by a small but consistent body of evidence. In brief, Pb exposure in
rats inhibits several enzymes involved in heme synthesis, most notably ALAD, the enzyme that catalyzes
the second, rate-limiting step in heme biosynthesis (Rendon-Ramirez et al.. 2007; Teravama et al.. 1986).
Pb exposure has also been shown to inhibit ferrochelatase, a mitochondrial iron (Fe)-sulfur (S) containing
enzyme that incorporates Fe2+into protoporphyrin IX to create heme (Rendon-Ramirez et al.. 2007).

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Toxicological studies have found that Pb exposures result in increases in markers of oxidative
stress. For example, Lee et al. (2005) reported increased RBC malondialdehyde (MDA), SOD and CAT
levels accompanied by significant decreases in GSH and GPx in rats exposed to Pb (25 mg/kg) once a
week for 4 weeks. In a second drinking water study performed in rats, administration of Pb acetate
(750 mg/kg in drinking water for 11 weeks) resulted in decreased concentrations of plasma Vitamin C,
Vitamin E, nonprotein thiol, and RBC-GSH, with simultaneous increased activity of SOD and GPx
(Kharoubi et al.. 2008). Effects on measures of oxidative stress were also observed in in vitro studies
including increased MDA and decreased SOD and CAT in RBCs (Ciubar et al.. 2007). and decreased
glutathione reductase (GR) activity in human RBCs (Coban et al.. 2007). and decreased GSH and
increased glutathione disulfide (GSSG).

There were no recent toxicology studies investigating the effects of Pb exposure on heme
synthesis that satisfied the PECOS criteria described in Section 7.2 available for this review.

7.4.3. Integrated Summary of Heme Synthesis

A small number of animal toxicological studies evaluated in the 2013 Pb ISA provide consistent
evidence that Pb exposures affect heme synthesis, including Pb-induced decreases in ALAD (Rendon-
Ramirez et al„ 2007; Terayama et al.. 1986) and ferrochelatase activities (Rendon-Ramirez et al.. 2007).
The toxicological evidence was supported by a larger body of ecotoxicological studies that demonstrate
ALAD inhibition in Pb-exposed aquatic and terrestrial invertebrates and vertebrates (Sections 6.3.4.3,
6.4.5.2, 6.4.5.3, and 6.4.15.2 of the 2013 Pb ISA). Ecological evidence from previous reviews
consistently observed Pb-induced ALAD inhibition in multiple species, including birds and fish (U.S.
EPA, 2013, 2006). Some cross-sectional epidemiologic studies evaluated in previous reviews provide
supporting evidence that concurrent BLLs are associated with decreased ALAD and ferrochelatase
activities in both adults and children. The majority of these studies, however, are limited by the lack of
rigorous methodology and consideration of potential confounding.

Recent evidence provided by epidemiologic and toxicological studies of Pb exposure and Hb
levels provides additional support for Pb-related impairment of heme synthesis. These studies are
discussed in more detail in Section 7.3.

7.5 Biological Plausibility

This section describes biological pathways that potentially underlie effects on hematology
measures resulting from exposure to Pb. Figure 7-1 depicts the proposed pathways as a continuum of
upstream events connected by arrows that may lead to downstream events observed in epidemiologic
studies. Evidence supporting these proposed pathways was derived from Sections 7.3 and 7.4 of this ISA,

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evidence reviewed in the 2013 Pb ISA (U.S. EPA. 2013). and recent evidence collected from studies that
may not meet the current PECOS criteria but contain mechanistic information supporting these pathways.
Discussion of how exposure to Pb may lead to hematological effects contributes to an understanding of
the biological plausibility of epidemiologic results. Note that the structure of the biological plausibility
section and the role of biological plausibility in contributing to the weight-of-evidence analysis used in
the 2013 Pb ISA are discussed below.

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Decreased Ca2+
/Mg2+ ATPase
activity

Altered hematopoiesis

ALAD = 5-aminolevulinic acid dehydratase; Ca2+ = calcium ion; Mg2+ = magnesium ion; RBC = red blood cell.

Note: The boxes represent the effects for which there is experimental or epidemiologic evidence related to Pb exposure, and the arrows indicate a proposed relationship between
those effects. Solid arrows denote evidence of essentiality as provided, for example, by an inhibitor of the pathway used in an experimental study involving Pb exposure. Dotted arrows
denote a possible relationship between effects. Shading around multiple boxes is used to denote a grouping of these effects. Arrows may connect individual boxes, groupings of
boxes, and individual boxes within groupings of boxes. Progression of effects is generally depicted from left to right and color coded (white, exposure; green, initial effect; blue,
intermediate effect; orange, effect at the population level or a key clinical effect). Here, population-level effects generally reflect results of epidemiologic studies. When there are gaps
in the evidence, there are complementary gaps in the figure and the accompanying text below. The structure of the biological plausibility sections and the role of biological plausibility
in contributing to the weight-of-evidence analysis used in the 2022 Pb ISA are discussed in Section 7.6.

Figure 7-1 Potential biological plausibility pathways for hematological effects associated with exposure to
Pb.

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Careful review of the available evidence indicates that exposure to Pb has the potential to
modulate the hematological parameters leading to decreased RBC survival and function and altered heme
synthesis. These deficits converge, promoting the development of anemia, a condition that occurs when
the number of RBCs and/or the concentration of Hb in RBCs is abnormally low. Below, evidence from
peer-reviewed toxicology studies providing biological plausibility for Pb-associated effects on
hematological parameters is reviewed.

7.5.1. Decreased Red Blood Cell Survival and Function

As described below, there is strong evidence that Pb impacts a series of hematological parameters
along a cascade of events that results in decreased RBC function and survival, possibly leading to anemia
(Figure 7-1). As reviewed in the 2013 Pb ISA, Pb uptake into human RBCs occurs through a passive
anion transport mechanism, and once Pb is in the cell, little leaves (Bcrgdahl et al.. 1997; Simons. 1993;
Simons. 1986). While the precise mechanisms responsible for decreasing RBC lifespan and mobility are
unknown, occupational Pb exposure has been shown to decrease intracellular free Ca+2 levels and
decrease Ca2+/Mg2+ ATPase activity in RBCs in workers (Abam et al.. 2008; Quintanar-Escorza et al..
2007). These changes are associated with fragility and morphological alterations in RBCs in Pb-exposed
workers. Pb-induced increases in intracellular Ca2+ levels also play a role in the activity of phospholipid
scramblases and flippases in RBCs, increasing access to PS by tissue macrophages and triggering splenic
sequestration and destruction of RBCs, leading to reduced numbers of RBCs in circulation (Jang et al..
2011). Importantly, Ahvavauch et al. (2018) showed that inhibiting Ca2+ increase stimulated by Pb results
in decreased flippase activity and prevented destruction of RBCs. This pathway is depicted in Figure 7-1
by solid lines linking increased intracellular Ca2+ to increased PS exposure and decreased RBC survival.
In addition, phagocytosis of Pb-exposed RBC by human renal proximal tubular cells was mediated by PS
(Kwon and Chung. 2016). Heme-regulated eIF2a kinase was shown to protect RBC from Pb-induced
hemolytic stress in mice (Wang et al.. 2015). Pb-induced hemolysis was also documented in other recent
studies (Hossain et al.. 2015; Mrugesh et al.. 2011). Furthermore, Pb exposure reduced the number of
RBCs and Hb levels in rats (Ibrahim et al.. 2012). Consistent with the pattern seen in epidemiology
studies, the effects of Pb exposure on RBC number and Hb level were more pronounced in 3-month-old
Wistar rats than in adult animals (Daku et al.. 2019). In addition, Cai et al. (2018) reported that Pb
administration reduced RBC lifespan in mice. These findings support the conclusion that Pb alters RBC
survival and function, consistent with the larger body of evidence showing measures of decreased
hematological parameters (i.e., RBC number, Hb, Hct, MCV, and/or MCH) in children (Guo et al.. 2021;
Kuang et al.. 2020; Li et al.. 2018; Liu et al.. 2015; Liu et al.. 2012) and animals (Odo et al.. 2020;
Andielkovic et al.. 2019; Cai et al.. 2018; Corsetti et al.. 2017; Lakshmi et al.. 2013; Berrahal et al.. 2011;
Sharma et al.. 2010; Wang et al.. 2010b; Baranowska-Bosiacka et al.. 2009; Masso-Gonzalez and
Antonio-Garcia. 2009; Simsek et al.. 2009; Masso et al.. 2007).

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Pb exposure also has the potential to disrupt normal hematopoiesis. Erythropoietin (EPO) is a
glycoprotein hormone excreted by the kidney to promote the development of RBCs in bone marrow. As
reviewed in the 2006 Pb AQCD, Pb exposure has been observed to alter EPO production in children
(Graziano et al., 2004; Factor-Litvak et al., 1999; Factor-Litvak et al., 1998). Available data support the
postulation that observed increases in EPO in younger children reflect bone marrow hyperactivity to
counteract RBC destruction, whereas the lack of EPO elevation in older children may reflect a transitional
period in which increasing renal and bone marrow toxicity leads to observed decreases in EPO later in
life (U.S. EPA, 2006). In addition to altering levels of a key hormone involved in hematopoiesis, Pb
exposure has the potential to alter hematopoiesis by causing cytotoxicity (Alghazal et al„ 2008; Marques
et al., 2006; Celik et al., 2005) and senescence (Cai et al., 2018; Nagano et al., 2015) of RBC precursors.
Baktybaeva (2011) reported that intraperitoneal injection of Pb acetate resulted in reduced bone marrow
hematopoiesis in mice. Furthermore, Pb is known to reduce erythropoiesis, causing anemia in children
(Dai et al„ 2017; Ahamed et al., 2011). Altered EPO levels and RBC precursor cytotoxicity have the
potential to alter the number of RBCs in circulation which may lead toto anemia.

7.5.2. Altered Heme Synthesis

Although the mechanisms that could lead to Pb-induced anemia are not fully understood, as
reviewed in the United States Environmental Protection Agency's (U.S. EPA's) 2006 Pb AQCD (U.S.
EPA, 2006), Pb is known to act directly on two enzymes involved in heme synthesis: ALAD and
ferrochelatase. ALAD, a cytoplasmic enzyme requiring zinc (Zn) for enzymatic activity, catalyzes the
rate-limiting step in heme biosynthesis. Inhibition of ALAD activity has been reported in adults (Wang et
al., 2010a) and children (Dai et al., 2017; Wang et al., 2010a; Ahamed et al., 2007) as well as in animal
toxicology studies reporting BLLs relevant to this ISA (i.e., 24.7 (ig/dL) (Rendon-Ramirez et al„ 2007;
Terayama et al., 1986). ALAD activity was also reduced in animal studies reporting BLLs higher than
those meeting the PECOS criteria in this ISA (Mani et al., 2020; Velaga et al., 2014; Whittaker et al.,
2011; Gautam and Flora, 2010; Lee et al., 2005). Pb exposure has also been shown to inhibit
ferrochelatase, a mitochondrial iron (Fe)-sulfur (S)containing enzyme that incorporates Fe2+into
protoporphyrin IX to create heme (Rendon-Ramirez et al., 2007). Pb inhibits the insertion of Fe2+into the
protoporphyrin ring and instead, Zn is inserted into the ring creating Zn-protoporphyrin (ZPP). Evidence
for altered heme synthesis is supported by a large body of evidence collected from occupationally
exposed adults (Ukaejiofo et al., 2009; Khan et al„ 2008; Patil et al., 2006; Karita et al., 2005), children
(Queirolo et al., 2010; Shah et al., 2010; Olivero-Verbel et al., 2007; Riddell et al., 2007), and Pb-exposed
experimental animal models (Andjelkovic et al„ 2019; Cai et al„ 2018; Berrahal et al., 2011;
Baranowska-Bosiacka et al., 2009; Masso-Gonzalez and Antonio-Garcia, 2009; Simsek et al., 2009;
Rendon-Ramirez et al., 2007; Marques et al., 2006; Terayama et al„ 1986) reporting decreased Hb
concentrations in association with Pb exposure or increased BLLs. Further demonstrating the role Pb

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plays in the activity of these important enzymes, chelation therapy restored ALAD activity and reduced
ZPP levels in blood harvested from rats exposed to Pb via drinking water for 90 days (Ata et al.. 2018).

Oxidative stress is caused by an imbalance between production and elimination of reactive
oxygen species (ROS) in cells or tissues that exceed the capacity of antioxidant defense mechanisms.
ROS are unstable, highly reactive molecules formed from molecular oxygen and include, for example,
superoxide (O2), hydroxyl radical (OH), and hydrogen peroxide (H2O2). Although ROS play an important
role in healthy biological systems (e.g., cell signaling, cellular differentiation, immune responses),
unregulated ROS can cause direct and indirect damage to nucleic acids, proteins, and lipids leading to
cytotoxicity, tissue injury, and even disruption of normal physiology (Auten and Davis. 2009). Oxidative
stress is involved in both arms of the pathway leading to anemia shown in Figure 7-1, including effects on
RBC MDA, SOD, CAT, GSH, and GPx levels (Kharoubi et al.. 2008; Lee et al.. 2005). Effects of Pb
exposure on measures of oxidative stress—including MDA and decreased SOD, CAT, GR, and GSSG—
were also observed in vitro (Ciubar et al.. 2007; Coban et al.. 2007).

Supporting the role of oxidative stress in the development of anemia, administration of
antioxidants reduced the effects of Pb exposure on levels of GSH (Alcaraz-Contreras et al.. 2011). MDA
(Alcaraz-Contreras et al.. 2011) and Hb (Farooq et al.. 2016; Saiitha et al.. 2016; Sarkar et al.. 2015;
Eshginia and Marjani. 2013) and reduced the effects of Pb exposure on SOD activity (Eshginia and
Mariani. 2013). ROS production (Nagano et al.. 2015; Sarkar et al.. 2015). hematopoietic stem cell (HSC)
number (Nagano et al.. 2015). HSC colony formation (Cai et al.. 2018). HSC senescence markers (Cai et
al.. 2018; Nagano et al.. 2015). RBC number (Farooq et al.. 2016; Saiitha et al.. 2016; Sarkar et al.. 2015).
and PS exposure (Sarkar et al.. 2015) in animal studies. Conflicting evidence on the effects of antioxidant
treatment on ALAD activity was reported in the literature (Saiitha et al.. 2016; Alcaraz-Contreras et al..
2011). whereas the evidence for effects of Pb exposure on Hb levels was consistent; thus, a solid arrow
connects oxidative stress to decreased RBC Hb content in Figure 7-1. Further demonstrating the role of
oxidative stress in the development of anemia, decreased ALAD activity results in the accumulation of
5-aminolevulinic acid (5-ALA) in blood and urine, where it undergoes tautomerization and autoxidation.

Oxidized 5-ALA leads to the generation of ROS (i.e., O2, OH, H2O2, and an aminolevulinic acid [ALA])
radicals (Hermes-Lima et al.. 1991; Monteiro et al.. 1991; Monteiro et al.. 1989; Monteiro et al.. 1986).
Reflecting the strength of the evidence described above, the pathway connecting oxidative stress to
altered hematopoiesis, cytotoxicity/senescence RBC precursor cells, and decreased RBC survival is
depicted as a solid line.

Decreased RBC Hb content and oxidative stress associated with Pb exposure have been
demonstrated to alter RBC function. This conclusion is supported by direct evidence for binding of Pb to
key enzymes in the heme synthesis pathway, Pb-induced oxidative stress resulting in decreased RBC Hb
content and effects on hematopoiesis, RBC precursor cells, and RBC survival. Decreased RBC number
coupled with impaired RBC function, if of sufficient magnitude, leads to Pb-induced anemia.

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7.6

Summary and Causality Determination

7.6.1. Causality Determination for Red Blood Cell Survival and Function

The 2013 Pb ISA presented causality determinations for two groups of hematological endpoints:
heme synthesis and RBC survival and function. Although there are enzymes and hematological
parameters that are distinct indicators of these processes, the potential biological plausibility pathways in
which exposure to Pb may result in hematological effects demonstrate a spectrum of events, which can be
challenging to attribute to a unique line of evidence (Figure 7-1). For example, altered heme synthesis can
decrease Hb levels, which in turn has been shown to alter RBC function. Because of this
interconnectedness, this assessment presents a single causality determination for Pb exposure and heme
synthesis and RBC survival and function. This approach allows for a more holistic evaluation of inter-
related health endpoints, including a discussion of how all individual lines of evidence contribute to the
overall causality determination. The key evidence, as it relates to the causal framework, is outlined below,
and summarized in Table 7-1.

7.6.2. Evidence for Red Blood Cell Survival and Function

The 2013 Pb ISA concluded that there is a "causal relationship" between Pb exposure and
decreased RBC survival and function (U.S. EPA. 2013). This causality determination was made on the
basis of a strong body of evidence from experimental animal studies demonstrating that Pb exposures
alter several hematological parameters (e.g., Hb, Hct, MCV, MCH), induce oxidative stress (e.g., alter
antioxidant enzyme activities [SOD, CAT, GPx], decrease cellular GSH, and increase lipid peroxidation),
and increase cytotoxicity in RBC precursor cells in rodents exposed to various forms of Pb via drinking
water and gavage resulting in BLLs <30 (ig/dL (Molina et al.. 2011; Baranowska-Bosiacka et al.. 2009;
Lee et al.. 2005). Consistent results were observed in several additional studies in rodents that did not
report BLLs. Epidemiologic evidence was coherent with results from the evaluated toxicological studies
but was subject to more uncertainties. Notably, the epidemiologic evidence consisted of cross-sectional
studies that were conducted in populations with higher mean Pb exposures (i.e., BLLs >10 |ig/dL). did
not thoroughly consider potential confounders, and lacked rigorous statistical methodology. These
limitations precluded strong conclusions on the directionality of effects; the level, timing, frequency, and
duration of Pb exposure that contributed to the observed associations; and whether the observed
associations are independent of potential confounders. Although there were substantial uncertainties in
the epidemiologic evidence, animal toxicological evidence established a clear basis for temporality of
exposure to Pb and effects on RBCs. Additional support for these findings was provided by toxicological
and epidemiologic studies demonstrating increased intracellular calcium concentrations, decreased
Ca2+/Mg2+ ATPase activity, and increased PS exposure, establishing biologically plausibility for Pb-
induced changes in RBC survival.

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Although limited in number, recent PECOS-relevant animal toxicological studies continue to
support the findings from the last review. The most consistent evidence comes from studies that report
decreased Hb levels in rodents following Pb exposures, resulting in BLLs ranging from 7.5 to 14.7 (ig/dL
(Andielkovic et al.. 2019; Cai et al.. 2018; Berrahal et al.. 2011). Other recent toxicological studies noted
Pb-induced decrements in Hct (Andielkovic et al.. 2019). packed cell volume (PCV) (Berrahal et al..
2011). and hematopoiesis (Andielkovic et al.. 2019). Recent epidemiologic studies expand on the
evidence presented in the 2013 Pb ISA and are coherent with the experimental evidence. Although the
recent studies are also cross-sectional, they include populations with much lower BLL means (<10 (ig/dL)
and include more robust adjustment for potential confounding, addressing important uncertainties from
the last review. The most consistent epidemiologic evidence indicates an inverse association between
BLLs and Hb levels in children (Section 7.3.1), which is in line with the evidence from recent
experimental animal studies. While the clinical relevance of small mean decrements in Hb across
exposure quintiles is unclear, a few of the recent epidemiologic studies observed higher odds of prevalent
anemia in children associated with higher quantiles of BLLs (Guo et al.. 2021; Li et al.. 2018). Recent
epidemiologic studies of Hb in adults were more limited in number and less consistent than those in
children. Additionally, the relatively few studies examining RBC counts were also inconsistent.

7.6.3. Evidence for Heme Synthesis

The 2013 Pb ISA concluded there is a "causal relationship" between Pb exposure and altered
heme synthesis (U.S. EPA, 2013). This determination was based on a small but consistent body of studies
in adult animals reporting that Pb exposures via drinking water and gavage (resulting in BLLs relevant to
this ISA) for 15 days to 9 months decreased ALAD (Rendon-Ramirez et al.. 2007; Terayama et al.. 1986)
and ferrochelatase activities (Rendon-Ramirez et al.. 2007). Notably, Rendon-Ramirez et al. (2007)
observed effects on ALAD and ferrochelatase activities in albino Wistar rats at mean BLLs of 24.7 (ig/dL
after Pb administration drinking water for 15 or 30 days. Supporting this toxicological evidence was a
larger body of ecotoxicological studies that demonstrate altered heme synthesis in Pb-exposed aquatic and
terrestrial invertebrates and vertebrates. Ecological evidence from previous reviews consistently observed
Pb-induced ALAD inhibition in multiple species, including birds and fish (U.S. EPA, 2013, 2006). Cross-
sectional epidemiologic studies provided supporting evidence that concurrent elevated BLLs are
associated with lower ALAD and ferrochelatase activities in both adults and children. However, the
majority of these studies are limited by the lack of rigorous methodology and consideration of potential
confounding. Although there were limitations in the epidemiologic evidence, some studies in children did
control for or consider potential confounding, and effects in adults and children in these studies are
coherent with effects observed in animal toxicological studies.

The relationship between Pb exposure and altered heme synthesis was further supported by cross-
sectional epidemiologic studies indicating an inverse association between BLLs and Hb in children and
occupationally exposed adults. These findings were consistent with several toxicological studies that

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observed decreased Hb levels in laboratory animals exposed to Pb. Decreased Hb levels can be a direct
indicator of decreased heme synthesis.

Recent PECOS-relevant studies are limited in number and focus mainly on Hb levels but continue
to provide support for Pb-related alterations in heme synthesis. Notably, recent epidemiologic studies
indicating an association between higher BLLs and lower Hb include more robust statistical methods,
expanded consideration of potential confounders, and populations with much lower BLLs than the studies
included in the previous reviews (mean or median BLLs ranging from 3.04 to 8.38 (ig/dL; Section 7.3.1).
The recent epidemiologic evidence is coherent with recent toxicological studies, which observed Hb
decrements in Pb-exposed mice (Andielkovic et al.. 2019; Cai et al.. 2018). While the cross-sectional
nature of the epidemiologic studies introduces uncertainty about the temporality of the exposure and
outcome, animal toxicological evidence establishes clear temporality of exposure to Pb and altered heme
synthesis.

7.6.4. Causality Determination

In summary, there is sufficient evidence to conclude that there is a causal relationship
between Pb exposure and hematological effects, including altered heme synthesis and decreased
RBC survival and function. The strongest support for this causality determination comes from
experimental animal studies demonstrating that exposures to various forms of Pb via drinking water or
gavage resulting in BLLs < 30 (ig/dL, alter several hematological parameters (e.g., Hb, Hct, MCV, MCH)
and decrease ALAD and ferrochelatase activities in rodents. These toxicology results are coherent with
findings from epidemiologic studies that report Pb exposures alter key hematological parameters and
enzymes. Although all evaluated epidemiologic studies are cross-sectional, toxicological studies establish
temporality between exposure to Pb and effects on heme synthesis and RBCs. Additionally, recent
epidemiologic studies address uncertainties from previous reviews by expanding adjustment for potential
confounders and using more robust statistical methods (i.e., multivariable regression models). Because of
the contribution of bone Pb levels to concurrent BLLs, associations with concurrent BLLs may reflect an
effect of past and/or recent Pb exposures. Therefore, there is uncertainty regarding the timing, duration,
and level of Pb exposure associated with observed hematological effects in children and adults. Biological
plausibility for the observed associations is provided by toxicological and epidemiologic studies
demonstrating increased intracellular calcium concentrations, decreased Ca2+/Mg2+ ATPase activity, and
increased PS exposure, which collectively can lead to fragility, morphological alterations in RBCs, and
RBC destruction.

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Table 7-1 Summary of evidence indicating a causal relationship between Pb exposure and hematological
effects

Rationale for Causality
Determination3

Key Evidence"

Key References"

Pb Biomarker Levels Associated
with Effects0

Red Blood Cell Survival and Function

Large body of studies with generally
consistent findings for decreased RBC
survival and function in rodents:

See Section 7.3.2

Mean BLLs (±SD):

Decreased plasma Hb concentration

Cai etal. (2018)

9.3 ± 0.98 |jg/dL

Consistent evidence from
toxicological studies with
relevant exposures

Andielkovic et al. (2019)

Berrahal etal. (2011)

Sharma et al. (2010)

Masso-Gonzalez and Antonio-Garcia

(2009)

Baranowska-Bosiacka et al. (2009)

29.0 ± 43.1 |jg/dL

12.67 ±1.68 |jg/dL PND 40;
7.49 ± 0.78 |jg/dL PND 65

1.72 ± 0.02 |jg/dL
22.8 ± 0.50 |jg/dL
7.11 ± 1.7 |jg/dL

Decreased Hct

Andielkovic et al. (2019)

Masso et al. (2007)

29.0 ± 14.7 |jg/dL
22.8 ± 0.50 |jg/dL

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Rationale for Causality
Determination3

Key Evidence"

Key References"

Pb Biomarker Levels Associated
with Effects0

Decreased RBCs

Decreased PCV

Increased eryptosis

Decreased hematopoiesis

Increased oxidative stress

Masso-Gonzalez and Antonio-Garcia
(2009)

Berrahal etal. (2011)

Andielkovic et al. (2019)
Cai etal. (2018)

Sharma et al. (2010)

U.S. EPA (2013)

U.S. EPA (2013)
U.S. EPA (2006)

U.S. EPA (2013)
U.S. EPA (2006)

In vitro:

Ciubar et al. (2007)
Coban et al. (2007)

22.8 ± 0.50 |jg/dL

12.67 ±1.68 |jg/dL PND 40;
7.49 ± 0.78 |jg/dL PND 65

29.0 ± 14.7 |jg/dL
9.3 ± 0.98 |jg/dL
1.72 ± 0.02 |jg/dL

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Rationale for Causality
Determination3

Key Evidence"

Key References"

Pb Biomarker Levels Associated
with Effects0

Shin etal. (2007)

Consistent evidence from
multiple epidemiologic
studies of children with
relevant BLLs provides
coherence with
toxicological evidence.

Cross-sectional studies provide support for
experimental evidence with consistent
associations between blood Pb and
decreased in Hb in children. Recent studies
adjusted for a number of relevant potential
confounders, including age, sex, BMI,
factors, and nutrition.

Guo et al. (2021)
Kuanq et al. (2020)
Li etal. (2018)
Liu etal. (2015)
Liu etal. (2012)

Mean BLLs:

3.07-3.21 |jg/dL

3.04 |jg/dL

8.38 |jg/dL (Median)

7.33 |jg/dL

4.30 |jg/dL (Median)

Cross-sectional studies provide generally U.S. EPA (2013)

consistent evidence for associations between

blood Pb and altered hematological

parameters (e.g., RBC counts, Hct, MCV, and

MCH), measures of oxidative stress

(e.g., SOD, CAT, GPx, GSH, and lipid

peroxidation), and hematopoiesis

(e.g., decreased erythropoietin). Evidence

base limited by lack of adjustment for potential

confounders and populations with higher

BLLs.

Biological Plausibility

Altered RBC membrane ion Evidence of increased [Ca2+]i and decreased See Section 7.5.2
transport	Ca2+/Mg2+ATPase activity in the RBCs of

exposed workers. [Ca2+]i levels highly
correlated with blood Pb even among
unexposed controls.

7-22


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Key References"

Pb Biomarker Levels Associated
with Effects0

Rationale for Causality
Determination3

Key Evidence"

Altered RBC membrane ion
transport

[Ca2+]i levels increased in RBCs from healthy
volunteers when exposed in vitro to Pb.

[Ca2+]i associated with increased RBC fragility
and alterations in RBC morphology.

PS exposure	Consistent evidence from in vivo and in vitro

studies that Pb exposure increases PS
exposure on RBC membranes via modulation
of[Ca2+]i concentrations. Increased PS
exposure leads to eryptosis and phagocytosis
by macrophages.

Heme Synthesis

Consistent evidence in
animals with relevant
exposures

A small, but consistent toxicology evidence
base indicates decreased heme synthesis in
rodents with relevant Pb concentrations and
routes of exposure.

Rendon-Ramirez et al. (2007)

BLL: 24.7 ± 2.4 pg/dL

Exposures: 500-5,000 ppm in drinking
water, 15-30 days as adults

Teravama et al. (1986)

Coherence in a limited
number of epidemiologic
studies with relevant BLLs

Cross-sectional studies that considered
potential confounding by age, sex, urban/rural
residence, height, weight, BMI found
consistent associations with lower ALAD and
ferrochelatase activities in children.

Ahamed et al. (2006)

Ahamed et al. (2007)

Mean BLL: 7.40 and 13.27 pg/dL

BLL: >10 pg/dL compared with
<10 pg/dL

Concurrent BLL associated with lower ALAD Wang et al. (2010a)
and higher ZPP in adults with consideration
for potential confounding by age, sex, smoking
status, and alcohol use.

Mean BLL: 6.71 pg/dL

7-23


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Rationale for Causality
Determination3

Key Evidence"

Key References"

Pb Biomarker Levels Associated
with Effects0

Support from toxicological Consistent evidence in animals with relevant Baranowska-Bosiacka et al. (2009).

and epidemiologic
evidence for decreases in
Hb, a direct marker of
decreased heme synthesis

Pb exposures for decreases in Hb levels.

Sharma et al. (2010)
Section 7.4.2

Consistent associations between concurrent
BLLs and decreased Hb in children.
Associations observed at low BLLs with
thorough consideration of potential
confounders.

Guo et al. (2021)
Kuana et al. (2020)
Li et al. (2018)
Liu et al. (2015)
Liu et al. (2012)

Adult animals: BLL7.11 ± 1.7 pg/dL
after 9-mo Pb exposure

Adult animals: BLL 1.7 pg/dL after 40-
day Pb exposure

Mean BLLs:

3.07-3.21 pg/dL

3.04 pg/dL

8.38 pg/dL (Median)

7.33 pg/dL

4.30 pg/dL (Median)

Biological Plausibility	Altered Ion Status: Evidence that Pb	See Section 7.5.2

competitively inhibits the binding ofZn ions
necessary for ALAD activity. Pb also inhibits
the incorporation of Fe2+ into protoporphyrin IX
by ferrochelatase, resulting in Zn-
protoporphyrin production.

ALAD = 6-aminolevulinic acid dehydratase; BLL = blood lead level; BMI = body mass index; Ca2+ = calcium ion(s); CAT = catalase; Fe2+ = iron; GPx = glutathione peroxidase;
GSH = glutathione; Hb = hemoglobin; Hct = hematocrit; i = inorganic; MCV = mean corpuscular volume; Mg2+ = magnesium; Pb = lead; PCV = packed cell volume; PND = postnatal
day; PS = phosphatidylserine; RBC = red blood cell; SES = socioeconomic status; SOD = superoxide dismutase; Zn = zinc; ZPP = Zn-protoporphyrin.

"Based on aspects considered in judgments of causality and weight of evidence in causal framework in Table I and Table II of the Preamble to the ISAs (U.S. EPA. 2015).
'Describes the key evidence and references, supporting or contradicting, contributing most heavily to causality determination and, where applicable, to uncertainties or
inconsistencies. References to earlier sections indicate where the full body of evidence is described.

Describes the Pb biomarker levels at which the evidence is substantiated.

7-24


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7.7 Evidence Inventories—Data Tables to Summarize Study Details

Table 7-2 Epidemiologic studies of exposure to Pb and hematological effects

Reference and
Study Design

Study Population

Exposure Assessment

Outcome

Confounders

Effect Estimates and
95% Clsa

Children

tGuoetal. (2021)

Guangdong Women and
Children's Hospital

Blood

Hb

Age and sex

Hb

Mean Difference (g/L)

Guangdong
China
2014-2017
Cross-sectional

n: 17,486

Children 0-5 yr old visiting
hospital for routine health
examination

BLLs were measured using
atomic absorption
spectrometry

Age at Measurement:
0-5 yr

Hb (g/L) measured
using an automated
hematology analyzer

Age at Outcome:
0-5 yr



Q1 (<1.61)
Reference
Q2 (1.61-2.44)
-0.05 (-0.51, 0.40)
Q3 (2.44-3.33)
-0.02 (-0.48, 0.43





Means:

Males: 3.21 |jg/dL;
Females: 3.07 |jg/dL





Q4 (3.33-4.50)









-0.48 (-0.94, -0.04)

Q5(>4.50)

-1.25 (-1.71, -0.78)

Anemia (OR)

Q1 (<1.61)
Reference
Q2 (1.61-2.44)

1.08 (0.94, 1.23)
Q3 (2.44-3.33)
1.16 (1, 1.33)
Q4 (3.33-4.50)
1.25 (1.07, 1.43)
Q5(>4.50)

7-25


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Reference and
Study Design

Study Population

Exposure Assessment

Outcome

Confounders

Effect Estimates and
95% Clsa

1.45 (1.26, 1.67)

tKuana et al. (2020) n: 395

Nanjing

China

2012

Cross-sectional

Convenience sample of
children 7-11 yr old

Blood

Blood Pb was measured in
venous whole blood using
ICP-MS

Age at Measurement:
7-11 yr old

Mean: 3.04 |jg/dL;

Median: 2.61 |jg/dL

Hematological
Parameters

RBC, Hb, Hct, MCV,
MCH, and MCHC
measured by a whole
cell analyzer

Age at Outcome:
7-11 yr old

Picky eaters and
passive smoking (age,
gender, parents'
education, and parents'
occupation also
considered)

RBC Count (1012/L)

Boys: 0.02 (-0.01, 0.04)
Girls: 0.01 (-0.02, 0.03)
Hb (g/L)

Boys:-0.12 (-0.22,
-0.02)

Girls: -0.08 (-0.23, 0.07)
Hct (%)

Boys: -0.04 (-0.08,
-0.01)

Girls: -0.02 (-0.07, 0.02)
MCV (fL)

-0.04 (-0.06, -0.02)
MCH (pg)

-0.01 (-0.02, -0.00)
MCHC (g/L)

0.26 (-0.64, 1.15)

tLiuetal. (2012)

China Jintan Child Cohort
Study

Blood

Hb

Age, sex, height,
weight, iron deficiency

Hb (g/dl_)*

Full Population

Changzhou City

n: 140

Blood Pb was measured in

Hb measured in whole



-0.096 (-0.18, -0.012)

China



whole blood using GFAAS

blood using a



Blood Pb < 10 ijg/dL

Cross-sectional

Convenience sample of
preschool age children

Age at Measurement:
Median age: 3 yr old

Median: 4.3 |jg/dL
Maximum: 11.4 pg/dL

photoelectric
colorimeter

Age at Outcome:
Median age: 3 yr old



-0.174 (-0.27, -0.078)

7-26


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Reference and
Study Design

Study Population

Exposure Assessment

Outcome

Confounders

Effect Estimates and
95% Clsa

tLi etal. (2018)

Hubei and Hunan
Provinces

China

2012-2017

Cross-sectional

Blood Lead Intervention
Program

n: 758

Children Ages 5-8 yr
recruited from four counties
in two provinces
One county in each province
had high environmental Pb
levels (battery plant and
mining)

Blood

Blood Pb was measured in
venous whole blood using
GFAAS

Age at Measurement:
5-8 yr

Median: 8.38 |jg/dL
75th: 13.51 pg/dL
90th: 18.77 pg/dL
95th: 21.82 pg/dL

Hematological
Parameters

Hb, MCH, RBCs, and
Pits measured in
venous whole blood
using an automated
hematology analyzer

Age at Outcome:
5-8 yr

Age, sex, BMI,
environmental Pb
exposure level, and
serum iron, zinc, and
calcium

ORs

Decreased Hb (<115 g/L)
1.05 (1.00, 1.11)
Decreased RBC
(<4 x 1012/L for boys;
<3.5 x 1012/L for girls)
1.11 (1.05, 1.16)
Decreased Pit
(<100 x 109/L)

1.11 (1.05, 1.16)
Decreased MCH (<27 pg)
1.11 (1.05, 1.16)

tLiuetal. (2015)

n: 855

Blood

Hb Age, sex, residence
area, and SES

Hb (g/L)

Mean Difference

Guiyu, Chendian,

Children 3-7 yr old from e-

Blood Pb was measured

Hb, MCH, RBCs, and

Q1 (5.98-13.52)*

and Chaonan

waste processing area or

using GFAAS. Blood Pbwas

Pits measured in

Reference

China

control industrial areas

divided by Hct as a fraction of

venous whole blood

Q2 (13.52-19.35)*

2006-2011

without high environmental

the whole blood to estimate

using an automated

Pb exposures

erythrocyte Pb

hematology analyzer

-0.02 (-1.89, 1.52)

Cross-sectional







Q3 (19.35-28.42)*





Age at Measurement:

Age at Outcome:

-3.01 (-4.71, 1.31)





3-7 yr old

3-7 yr old

Q4 (28.42-101.01)*
-3.97 (-5.68, -2.27)





Median:









Blood Pb: 7.33 pg/dL;



*Erythrocyte Pb (pg/dL)





Erythrocyte Pb: 19.3 pg/dL





Adults

7-27


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Reference and
Study Design

Study Population

Exposure Assessment

Outcome

Confounders

Effect Estimates and
95% Clsa

tPark and Lee
(2013)

South Korea

2008-2010

Cross-sectional

KNHANES
n: 4522

General population, >20 yr
old

Blood

Blood Pb was measured in
venous whole blood using
GFAAS

Age at Measurement:
>20 yr

Geometric Means:

Males: 2.46 |jg/dL;
Females: 1.98 |jg/dL

Hb

Blood Hb (g/dL)
measured using an
automated hematology
analyzer

Age at Outcome:
>20 yr

Age, BMI, education, Hb (g/dL)*

smoking and drinking
status, and rural/urban
residence

Men

0.04 (0.03, 0.06)
Women

0.04 (0.02, 0.06)

*Not standardized.
In(Pb) increase

Per

tKim and Lee
(2013)

South Korea

2008-2010

Cross-sectional

KNHANES
n: 5951

General population, >20 yr
old

Blood

Blood Pb was measured in
whole blood using GFAAS.
Blood Pb was divided by Hct
as a fraction of the whole
blood to estimate erythrocyte
Pb

Age at Measurement:
>20 yr old

Median:

Blood Pb: 2.31 pg/dL;
Erythrocyte Pb: 5.4 pg/dL
75th:

Blood Pb: 3.01 pg/dL;
Erythrocyte Pb: 6.9 pg/dL

Hb

Hb measured in whole
blood using an
automated hematology
analyzer

Age at Outcome:
>20 yr old

Sex, age, obesity,
residence area,
education level,
smoking and drinking
status, serum ferritin,
and serum creatinine

Hb (g/L)

Mean Difference
Q1 (<1.73)
Reference
Q2 (1.73-2.31)
0.13 (0.03, 0.23)
Q3 (2.31-3.01)
0.33 (0.23, 0.42)
Q4 (>3.01)
0.42 (0.30, 0.53)

Q1 (<4.1)*
Reference
Q2 (4.1-5.4)
-0.06 (0.15, 0.03)
Q3 (5.4-6.9)
-0.06 (-0.15, 0.03)
Q4 (>6.9)

-0.14 (-0.25, -0.04)

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Reference and
Study Design

Study Population

Exposure Assessment

Outcome

Confounders

Effect Estimates and
95% Clsa

*Erythrocyte Pb (pg/dL)

tLa-Llave-Leon et n: 292
al. (2015)

Durango
Mexico
2007-2008
Cross-Sectional

Pregnant women, 14-41 yr
old

Blood

Blood Pb was measured in
venous whole blood using
GFAAS

Age at Measurement:
14-41 yr old

Hematological
Parameter

RBC, Hb, Hct, MCV,
MCH, and MCHC
measured using an
automated hematology
analyzer

BMI, gestational age,
age, parity, gestations,
and household monthly
income per person

RBC Count (x106Mg/dL)

0.034 (0.013, 0.056)

Mean: 2.79 |jg/dL

Age at Outcome:
14-41 yr old

BMI = body mass index; BW = body weight; CI = confidence interval; e-waste = electronic waste; GFAAS = graphite furnace atomic absorption spectrometry; Hb = hemoglobin;
Hct = hematocrit; ICP-MS = inductively coupled plasma mass spectrometry; KNHANES = Korea National Health and Nutrition Examination Survey; In = natural log; MCH = mean
corpuscular hemoglobin; MCHC = mean corpuscular hemoglobin concentration; MCV = mean corpuscular volume; OR = odds ratio; Pb = lead; Pit = platelet; PND = postnatal day;
Q = quartile; RBC = red blood cell; RDW = red blood cell distribution width; SES = socioeconomic status; yr = year(s).

aEffect estimates are standardized to a 1 |jg/dL increase in blood Pb level or a 10 |jg/g increase in bone Pb level, unless otherwise noted. For studies that report results
corresponding to a change in log-transformed Pb biomarkers, effect estimates are assumed to be linear within the 10th to 90th percentile interval of the biomarker and standardized
accordingly.

fStudies published since the 2013 Pb ISA.

7-29


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Table 7-3 Animal toxicological studies of Pb exposure and hematological effects

Study (StolEin), n, Timing of	Exposure Details	BLL as Reported (pg/dL)3

' v Sex '	Exposure	(Concentration, Duration)	^ VMa '	Examined

Berrahal et Rat (Wistar)

al. (2011)

Control (vehicle),
M,n = 12-16

50 mg/L Pb, M,
n = 12-16

PND 1 to

PND21:

Lactational

PND 21 to
PND 40 or
PND 65:
Drinking water

Dams were given 50 mg/L Pb acetate in drinking PND 40:

Hct, Hb

water until weaning on PND 21. Male offspring
received 50 mg/L Pb acetate in drinking water
from PND 21 to PND 40 or PND 65. Control
animals received tap water.

1.76 ± 0.33 |jg/dL for 0 pg/dL
12.67 ± 1.68 pg/dL for 50 mg/L

PND 65:

2.06 ± 0.35 pg/dL for 0 pg/dL
7.49 ± 0.78 pg/dL for 50 mg/L

Basha et al. Rat (Wistar) PND 1
(2012)	Control (vehicle), *° P^D 21

M, n = 8

0.2% Pb, M, n = 8

PND 12 mo:

0.56 ± 0.08 pg/dL for 0%,
16.4 ± 1.95 pg/dL for 0.2%,
7.2 ± 0.56 pg/dL for 0.2% +
supplementation

Damns given Pb acetate in drinking water or Pb
acetate containing water supplemented with
0.02% calcium, zinc, and iron. Control group
received deionized water as vehicle (no
supplement).

Pups exposed through lactation.

PND 45:	RBC, Hb

0.42 ± 0.04 pg/dL for 0%,

52.5 ± 0.67 pg/dL for 0.2%,

21.1 ± 1.12 pg/dL for 0.2% +
supplementation

PND 24 mo:

0.46 ± 0.02 pg/dL for 0%,
12.2 ± 0.76 pg/dL for 0.2%,
4.8 ± 0.5 pg/dL for 0.2% for
0.2% + supplementation

Zou et al. Mouse (ICR)	3 wk exposure Rats received 250 mg/L Pb acetate in redistilled PND 58:	RBC, MCHC

(2015) Control (vehicle),	drinking water for 3 wk. The rats were 30 d old 1.8 pg/dL for 0 mg/L

m n-m	when acquired, but the authors did not specify

M'n"1°	the age at the time of treatment. 21.7 pg/dL for 250 mg/L

250 mg/L Pb, M,
n = 10

7-30


-------
Species

Timing of

Study (Stock/SJrain), n, ¦ —»-

Exposure Details
(Concentration, Duration)

BLL as Reported (|jg/dL)a

Endpoints
Examined

Corsetti et al. Mouse
(2017)	(C57BL.6)

Control (vehicle),
M, n = 8

d 30 to d 75 Mice were exposed via drinking water for 45

consecutive days. Control animals were exposed
to drinking water containing acetic acid (1 mL/L).

<5 |jg/dL for 0 ppm

21.6 |jg/dL for 200 ppm

RBC, Hb, Hct,
MCV, MCH,
MCHC, RDW %,
Pits

200 ppm Pb, M,
n = 8

Andielkovic Rat (Wistar) NR

et al. (2019) control (vehicle),
M, n = 8

0.2% Pb, M, n = 6

Rats (250 g), age at time of dosing not reported,
were exposed to a single dose of 150 mg Pb/kg
BW Pb acetate via oral gavage. Control animals
were given "water."

24.9 ± 1 9 |jg/kg for 0 mg Pb/kg BW
(2.6 ± 2.0 |jg/dL)

291.2 ± 139 |jg/kg for 150 mg Pb/kg
BW

(29.0 ± 14.7 |jg/dL)

RBC, Hb, Hct,
MCV, MCH,
MCHC, Pits

Cai et al.
(2018)

Rat (Sprague
Dawley)

Control (vehicle),
M/F, n = 5

0.2% Pb, M/F,
n = 5

8-10 wk to 20- Rats were 8-10 wk old when acquired. Whether
22 wk	or not the rats were allowed to acclimate to the

facility prior to study initiation was not reported.
The number of males and females not reported.

Control animals received tap water.

The exposure period was 12 wk, assumed rats
were exposed 7 d/wk for a total of 84 d.

20.5 ± 0.68 |jg/L for 0%
(2.2 ± 6.4 |jg/dL)
87.4 ± 9.2 |jg/L for 0.2%
(9.3 ± 0.98 |jg/dL)

Hb, Pits,
Erythrocyte life
span, RBC

BLL = blood lead level; BW = body weight; d = day; Hb = hemoglobin; Hct = hematocrit; M = male; M/F = male/female; MCH = mean corpuscular hemoglobin; MCHC = mean
corpuscular hemoglobin concentration; MCV = mean corpuscular volume; mo = month(s); NR = not reported; Pb = lead; Pit = platelet; PND = postnatal day; RBC = red blood cell;
RDW = red blood cell distribution width; wk = week(s).

alf applicable, reported values for BLL were converted to |jg/dL using WebPlot Digitizer (https://apps.automeris.io/wpd/) and are shown in parenthesis.

7-31


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7.8 References

Abam. E: Okediran. BS: Odukova. 00: Adamson. I; Ademuviwa. O. (2008). Reversal of ionoregulatory disraptions
in occupational lead exposure by vitamin C. Environ Toxicol Pharmacol 26: 297-304.
http://dx.doi.Org/10.1016/i.etap.2008.05.008.

Ahamed. M: Akhtar. MJ: Venna. S: Kumar. A: Siddiaui. MKJ. (2011). Environmental lead exposure as a risk for
childhood aplastic anemia. 5: 38-43. http://dx.doi.Org/10.5582/bst.2011.v5.l.38.

Ahamed. M: Singh S: Behari. JR: Kumar. A: Siddiaui. MKJ. (2007). Interaction of lead with some essential trace
metals in the blood of anemic children from Lucknow, India. Clin Cliim Acta 377: 92-97.
http://dx.doi.Org/10.1016/i.cca.2006.08.032.

Ahamed. M: Venna. S: Kumar. A: Siddiaui. MKJ. (2006). Delta-aminolevulinic acid dehydratase inhibition and
oxidative stress in relation to blood lead among urban adolescents. Hum Exp Toxicol 25: 547-553.
http://dx.doi.org/10.1191/0960327106het657oa.

Ahvavauch H: Garcia-Arribas. AB: Sot. J: Gonzalez-Ramirez. EJ: Busto. JV: Monasterio. BG: Jimenez-Roio. N:
Contreras. FX: Rendon-Ramirez. A: Martin. C: Alonso. A: Gofii. FM. (2018). Pb(II) induces scramblase
activation and ceramide-domain generation in red blood cells. Sci Rep 8: 7456.
http://dx.doi.org/10.1038/s41598-018-25905-8.

Alcaraz-Contreras. Y: Garza-Ocafias. L: Carcafio-Diaz. K: Ramirez-Gomez. XS. (2011). Effect of glycine on lead
mobilization, lead-induced oxidative stress, and hepatic toxicity in rats. J Toxicol 2011: 430539.
http://dx.doi.org/10.1155/2011/430539.

Alghazal. MA: Sutiakova. I: Kovalkovicova. N: Legath. J: Falis. M: Pistl. J: Sabo. R: Benova. K: Sabova. L: Vaczi.
P. (2008). Induction of micronuclei in rat bone marrow after chronic exposure to lead acetate trihydrate.
Toxicol IndHealth 24: 587-593. http://dx.doi.org/10.1177/0748233708100Q89.

Andielkovic. M: Diordievic. AB: Antoniievic. E: Antoniievic. B: Stanic. M: Kotur-Stevulievic. J: Spasoievic-

Kalimanovska. V: Jovanovic. M: Boricic. N: Wallace. D: Bulat. Z. (2019). Toxic effect of acute cadmium
and lead exposure in rat blood, liver, and kidney. Int J Environ Res Public Health 16: 274.
http://dx.doi.org/10.3390/iierphl6020274.

Ata. SA: Abu-Dari. KI: Tutunii. MF: Mubarak. MS. (2018). Reversing the adverse biochemical effects in lead-
intoxicated rats by N.N - bis|( 1.2-didchvdro-1 -hvdro.\Y-2-thio.\opy rid-4-\i)-carbon\i |- L-lysine. J Trace
Elem Med Biol 50: 93-99. http://dx.doi.Org/10.1016/i.itemb.2018.06.008.

Auten. RL: Davis. JM. (2009). Oxygen toxicity and reactive oxygen species: the devil is in the details [Review].
Pediatr Res 66: 121-127. "http://dx.doi.org/10.1203/PDR.0b013e3181a9eafb.

Baktvbaeva. LK. (2011). [Effect of new compound BIV-30 on bone-marrow hemopoiesis under conditions of lead-
acetate-induced myelosuppression], Eksp KlinFannakol 74: 26-28.

Baranowska-Bosiacka. I: Dziedzieiko. V: Safranow. K: Gutowska. I: Marchlewicz. M: Dolegowska. B: Rac. ME:
Wiszniewska. B: Chlubek. D. (2009). Inhibition of erythrocyte phosphoribosyltransferases (APRT and
HPRT) by Pb2+: A potential mechanism of lead toxicity. Toxicology 259: 77-83.
http://dx.doi.Org/10.1016/i.tox.2009.02.005.

Basha. DC: Basha. SS: Reddv. GR. (2012). Lead-induced cardiac and hematological alterations in aging Wistar
male rats: alleviating effects of nutrient metal mixture. Biogerontology 13: 359-368.
http://dx.doi.org/10.1007/slQ522-012-9380-9.

Bergdahl. IA: Grubb. A: Schtitz. A: Desnick. RJ: Wetmur. JG: Sassa. S: Skerfving. S. (1997). Lead binding to 5-
aminolevulinic acid dehydratase (ALAD) in human erythrocytes. Basic Clin Pharmacol Toxicol 81: 153-
158. http://dx.doi.org/10". 1111/i. 1600-0773.1997.tb02061.x.'

7-32


-------
Berrahal. AA: Lasram. M: El Eli. N: Kerkeni. A: Gharbi. N: El-Fazaa. S. (2011). Effect of age-dependent exposure
to lead on hepatotoxicity and nephrotoxicity in male rats. Environ Toxicol 26: 68-78.
http://dx.doi.org/10.1002/tox.2053Q.

Cai. SZ: Zhou. Y: Liu. J: Li. CP: Jia. DY: Zhang. MS: Wang. YP. (2018). Alleviation of ginsenoside Rgl on
hematopoietic homeostasis defects caused by lead-acetate. Biomed Phannacother 97: 1204-1211.
http://dx.doi.Org/10.1016/i.biopha.2017.10.148.

CDC. (2019). Fourth national report on human exposure to environmental chemicals, updated tables, January 2019,
volume 1. https://stacks.cdc.gov/view/cdc/75822/cdc 75822 DSl.pdf.

Celik. A: Qgenler. O: Comelekoglu. U. (2005). The evaluation of micronucleus frequency by acridine orange
fluorescent staining in peripheral blood of rats treated with lead acetate. Mutagenesis 20: 411-415.
http://dx.doi.org/10.1093/mutage/gei055.

Ciubar. R: Ciofrangeanu. C: Mitran. V: Cimpean. A: Stanescu. A: Iordachescu. D. (2007). The effect of lead ions on
human erythrocytes in vitro. Rev Cliim 58: 895-897.

Coban. TA: Senturk. M: Ciftci. M: Kufrevioglu. 01. (2007). Effects of some metal ions on human erythrocyte
glutathione reductase: An in vitro study. Protein Pept Lett 14: 1027-1030.
http://dx.doi.org/10.2174/09298660778254106Q.

Corsetti. G: Romano. C: Stacchiotti. A: Pasini. E: Dioguardi. FS. (2017). Endoplasmic reticulum stress and

apoptosis triggered by sub-chronic lead exposure in mice spleen: A histopathological study. Biol Trace
ElemRes 178: 86-97. http://dx.doi.org/10.1007/sl2011-016-0912-z.

Dai. Y: Huo. X: Zhang. Y: Yang. T: Li. M: Xu. X. (2017). Elevated lead levels and changes in blood morphology
and erythrocyte CR1 in preschool children from an e-waste area. Sci Total Environ 592: 51-59.
http://dx.doi.Org/10.1016/i.scitotenv.2017.03.080.

Daku. AB: Mustapha. S: Salisu. AI: El-Ta'alu. AB. (2019). Age-related effects of lead poisoning on some
haematological parameters in adult wistar rats. Niger J Physiol Sci 34: 125-130.

Eshginia. S: Mariani. A. (2013). The effect of vitamin C on the erythrocyte antioxidant enzymes in intoxicated-lead
rat offsprings. JCDR 7: 1078-1081. http://dx.doi.org/10.7860/JCDR/2013/5310.3d59.

Factor-Litvak. P: Slavkovich. V: Liu. X: Popovac. D: Preteni. E: Capuni-Paracka. S: Hadzialievic. S: Lekic. V:

Lolacono. N: Kline. J: Graziano. J. (1998). Hyperproduction of erythropoietin in nonanemic lead-exposed
children. Environ Health Perspect 106: 361-364. http://dx.doi.org/10.1289/ehp.98106361.

Factor-Litvak. P: Wassennan. G: Kline. JK: Graziano. J. (1999). The Yugoslavia prospective study of

enviromnental lead exposure. Environ Health Perspect 107: 9-15. http://dx.doi.org/10.2307/3434284.

Farooq. Y: Farooq. MA: Hussain. A. (2016). Role of ascorbic acid supplement in amelioration of anaemia in lead
intoxication. J Pak Med Assoc 66: 1073-1076.

Gautam. P: Flora. SJS. (2010). Oral supplementation of gossypin during lead exposure protects alteration in heme
synthesis pathway and brain oxidative stress in rats. Nutrition 26: 563-570.
http://dx.doi.Org/10.1016/i.nut.2009.06.008.

Graziano. J: Slavkovich. V: Liu. XH: Factor-Litvak. P: Todd. A. (2004). A prospective study of prenatal and
childhood lead exposure and erythropoietin production. J Occup Environ Med 46: 924-929.
http://dx.doi.org/10.1097/01.iom.0000137721.95544.4f.

Guo. Y: Deng. YH: Ke. HJ: Wu. JL. (2021). Iron status in relation to low-level lead exposure in a large population
of children aged 0-5 years. Biol Trace Elem Res 199: 1253-1258. http://dx.doi.org/10.1007/sl2011-020-
02253-1.

Hermes-Lima. M: Pereira. B: Bechara. EJH. (1991). Are free radicals involved in lead poisoning? [Review].
Xenobiotica 21: 1085-1090. http://dx.doi.org/10.3109/00498259109Q39548.

Hossain. S: Bhowmick. S: Islam. S: Rozario. L: Jahan. S: Hassan. M: Sarkar. M: Choudhurv. BK: Ahmed. S:

Shahialal. H. (2015). Oral administration of Ganodenna lucidum to lead-exposed rats protects erythrocytes
against hemolysis: Implicates to anti-anemia. eCAM 2015: 463703. http://dx.doi.org/10.1155/2015/463703.

7-33


-------
Ibrahim. NM; Eweis. EA: El-Beltagi. HS: Abdel-Mobdv. YE. (2012). Effect of lead acetate toxicity on experimental
male albino rat. Asian Pacific Journal of Tropical Biomedicine 2: 41-46. http://dx.doi.org/10.lQ16/S2221-
1691(11)60187-1.

Jang. WH: Lim. KM: Kim. K: Noh. JY: Kang. S: Chang. YK: Chung. JH. (2011). Low level of lead can induce
phosphatidylserine exposure and erythrophagocytosis: A new mechanism underlying lead-associated
anemia. Toxicol Sci 122: 177-184. http://dx.doi.org/10.1093/toxsci/kfr079.

Karita. K: Yano. E: Dakeishi. M: Iwata. T: Murata. K. (2005). Benchmark dose of lead inducing anemia at the
workplace. Risk Anal 25: 957-962. http://dx.doi.org/10.1111/i. 1539-6924.2005.00652.X.

Khan DA: Oavvum. S: Saleem. S: Khan. FA. (2008). Lead-induced oxidative stress adversely affects health of the
occupational workers. Toxicol Ind Health 24: 611-618. http://dx.doi.org/10.1177/0748233708098127.

Kharoubi. O: Slimani. M: Krouf. D: Seddik. L: Aoues. A. (2008). Role of wormwood (Artemisia absinthium)

extract on oxidative stress in ameliorating lead induced haematotoxicity. African Journal of Traditional,
Complementary and Alternative Medicines 5: 263-270. http://dx.doi.org/10.4314/aitcam.v5i3.31282.

Kim. Y: Lee. BK. (2013). Increased erythrocyte lead levels correlate with decreased hemoglobin levels in the

Korean general population: Analysis of 2008-2010 Korean National Health and Nutrition Examination
Survey data. Int Arch Occup Environ Health 86: 741-748. http://dx.doi.org/10.1007/s00420-012-Q811-3.

Kuang. W: Chen Z: Shi. K: Sun. H: Li. H: Huang. L: Bi. J. (2020). Adverse health effects of lead exposure on
physical growth, erythrocyte parameters and school performances for school-aged children in eastern
China. Environ Int 145: 106130. http://dx.doi.Org/10.1016/i.envint.2020.106130.

Kwon. SY: Chung. JH. (2016). Erythrophagocytosis of lead-exposed erythrocytes by renal tubular cells may
contribute to lead-induced nephrotoxicity [Abstract]. Toxicol Lett 259(Suppl.): S239.
http://dx.doi.Org/10.1016/i.toxlet.2016.07.574.

La-Llave-Leon. O: Lugo-Soto. R: Aguilar-Duran. M: Estrada-Martinez. S: Salas-Pacheco. JM: Sandoval-Carrillo.
A: Castellanos-Juarez. FX: Barraza-Salas. M: Vazquez-Alanis. F: Garcia-Vargas. G. (2015). Relationship
between blood lead levels and hematological indices in pregnant women. Women Health 55: 90-102.
http://dx.doi.org/10.1080/03630242.2014.972Q19.

Lakshmi. BVS: Sudhakar. M: Aparna. M. (2013). Protective potential of Black grapes against lead induced
oxidative stress in rats. Environ Toxicol Pharmacol 35: 361-368.
http://dx.doi.Org/10.1016/i.etap.2013.01.008.

Lee. MK: Clio. SY: Kim. PJ: Jang. JY: Shin. KH: Park. SA: Park. EM: Lee. JS: Choi. MS: Lee. JS: Kim. M.T
(2005). Du-zhong (Eucommia ulmoides Oliv.) cortex water extract alters heme biosynthesis and
erythrocyte antioxidant defense system in lead-administered rats. J Med Food 8: 86-92.
http://dx.doi.Org/10.1089/imf.2005.8.86.

Lee. MY: Shin. JH: Han. HS: Chung. JH. (2006). In vivo effects of lead on erythrocytes following chronic exposure
through drinking water. Arch Phann Res 29: 1158-1163. http://dx.doi.org/10.1007/BF029693Q8.

Li. C: Ni. ZM: Ye. LX: Chen. JW: Wang. O: Zhou. YK. (2018). Dose-response relationship between blood lead
levels and hematological parameters in children from central China. Environ Res 164: 501-506.
http://dx.doi.Org/10.1016/i.envres.2018.03.018.

Liu. C: Huo. X: Lin. P: Zhang. Y: Li. W: Xu. X. (2015). Association between blood erythrocyte lead concentrations
and hemoglobin levels in preschool children. Environ Sci Pollut Res Int 22: 9233-9240.
http://dx.doi.org/10.1007/sll356-014-3992-3.

Liu. J: McCaulev. L: Yan. C: Shen. X: Pinto-Martin. JA. (2012). Low blood lead levels and hemoglobin
concentrations in preschool children in China. Toxicol Environ Chem 94: 423-426.
http://dx.doi.org/10.1080/02772248.2011.628Q01.

Mani. MS: Joslii. MB: Shettv. RR: Dsouza. VL: Swatlii. M: Kabekkodu. SP: Dsouza. HS. (2020). Lead exposure
induces metabolic reprogramming in rat models. Toxicol Lett 335: 11-27.
http://dx.doi.Org/10.1016/i.toxlet.2020.09.010.

7-34


-------
Marques. CC: Nunes. AC: Pinheiro. T: Lopes. PA: Santos. MC: Viegas-Crespo. AM: Ramalliinlio. MG: Matliias.
ML. (2006). An assessment of time-dependent effects of lead exposure in algerian mice (Mus spretus)
using different methodological approaches. Biol Trace Elem Res 109: 75-89.
http://dx.doi.Org/10.1385/BTER:109:l:075.

Masso-Gonzalez. EL: Antonio-Garcia. MT. (2009). Natural antioxidants protect against lead-induced damage during
pregnancy and lactation in rat's pups. Ecotoxicol Environ Saf 72: 2137-2142.
http://dx.doi.Org/10.1016/i.ecoenv.2009.03.013.

Masso. EL: Corredor. L: Antonio. MT. (2007). Oxidative damage in liver after perinatal intoxication with lead
and/or cadmium. J Trace Elem Med Biol 21: 210-216. http://dx.doi.Org/10.1016/i.itemb.2007.03.002.

Molina. RM: Phattanarudee. S: Kim. J: Thompson. K: Wessling-Resnick. M: Maher. TJ: Brain. JD. (2011).

Ingestion of Mn and Pb by rats during and after pregnancy alters iron metabolism and behavior in
offspring. Neurotoxicology 32: 413-422. http://dx.doi.Org/10.1016/i.neuro.2011.03.010.

Monteiro. HP: Abdalla. DSP: Augusto. O: Bechara. EJH. (1989). Free radical generation during 5-Aminolevulinic
acid autoxidation: Induction by hemoglobin and connections with porphyrinpathies. Arch Biochem
Biophys 271: 206-216. http://dx.doi.org/10.1016/0003-9861(89)90271-3.

Monteiro. HP: Abdalla. DSP: Falioni-Alario. A: Bechara. EJH. (1986). Generation of active oxygen species during
coupled autoxidation of oxyhemoglobin and 5-aminolevulinic acid. Biochim Biophys Acta 881: 100-106.
http://dx.doi.org/10.1016/0304-4165(86)90102-9.

Monteiro. HP: Bechara. EJH: Abdalla. DSP. (1991). Free radicals involvement in neurological porphyrias and lead
poisoning [Review]. Mol Cell Biochem 103: 73-83. http://dx.doi.org/10.1007/BF0Q229595.

Mrugesh. T: Dipa. L: Manishika. G. (2011). Effect of lead on human erythrocytes: An in vitro study. Acta Pol
Phann 68: 653-656.

Nagano. S: Takahashi. Y: Yamamoto. K: Masutani. H: Fuiiwara. N: Liu. J: Jia. D: Cai. S: Li. CP: Zhang. MS:

Zhang. Y: Yan. CH: Wang. YP. (2015). Mitochondria defects are involved in lead-acetate-induced adult
hematopoietic stem cell decline. Toxicol Lett 235: 37-44. http://dx.doi.Org/10.1016/i.toxlet.2015.03.007.

Odo. RI: Mbegbu. EC: Anvanwu. LN. (2020). Effect of aqueous ginger (Zingiber officinale) extract on sperm
quality and haematology in lead acetate-treated male albino rats. Tropical Journal of Pharmaceutical
Research 19: 1481-1485. http://dx.doi.org/10.4314/tipr.vl9i7.21.

Olivero-Verbel. J: Duarte. D: Echenique. M: Guette. J: Johnson-Restrepo. B: Parsons. PJ. (2007). Blood lead levels
in children aged 5-9 years living in Cartagena, Colombia. Sci Total Environ 372: 707-716.
http://dx.doi.Org/10.1016/i.scitotenv.2006.10.025.

Park. S: Lee. BK. (2013). Body fat percentage and hemoglobin levels are related to blood lead, cadmium, and

mercury concentrations in a Korean adult population (KNHANES 2008-2010). Biol Trace Elem Res 151:
315-323. http://dx.doi.org/10.1007/sl2011-Q12-9566-7.

Patil. AJ: Bhagwat. VR: Patil. JA: Dongre. NN: Ambekar. JG: Jailkhani. R: Das. KK. (2006). Effect of lead (Pb)

exposure on the activity of superoxide dismutase and catalase in battery manufacturing workers (BMW) of
Western Maharashtra (India) with reference to heme biosynthesis. Int J Environ Res Public Health 3: 329-
337. http://dx.doi.org/10.3390/iierpli2006030Q41.

Oueirolo. EI: Ettinger. AS: Stoltzfus. RJ: Kordas. K. (2010). Association of anemia, child and family characteristics
with elevated blood lead concentrations in preschool children from Montevideo, Uruguay. Arch Environ
Occup Health65: 94-100. http://dx.doi.org/10.1080/1933824090339Q313.

Ouintanar-Escorza. MA: Gonzalez-Martinez. MT: Navarro. L: Maldonado. M: Arevalo. B: Calderon-Salinas. JV.
(2007). Intracellular free calcium concentration and calcium transport in human erythrocytes of lead-
exposed workers. Toxicol Appl Pharmacol 220: 1-8. http://dx.doi.Org/10.1016/i.taap.2006.10.016.

Rendon-Ramirez. A: Cerbon-Solorzano. J: Maldonado-Vega. M: Ouintanar-Escorza. MA: Calderon-Salinas. JV.
(2007). Vitamin-E reduces the oxidative damage on 5-aminolevulinic dehydratase induced by lead
intoxication in rat erythrocytes. Toxicol In Vitro 21: 1121-1126.
http://dx.doi.Org/10.1016/i.tiv.2007.04.019.

7-35


-------
Riddell. TJ: Solon. Q: Ouimbo. SA: Tan. CMC: Butrick. E: Peabodv. JW. (2007). Elevated blood-lead levels among
children living in the rural Philippines. Bull World Health Organ 85: 674-680.
http://dx.doi.org/10.2471/blt.06.Q36137.

Saiitha. GR: Augusti. KT: Jose. R. (2016). Prophylactic effects of garlic oil and onion oil fractions as compared to
vitamin E on rats orally fed with lead acetate solution. Indian J Clin Biochem 31: 260-269.
http://dx.doi.org/10.1007/sl2291-015-Q526-9.

Sarkar. A: Sengupta. D: Mandal. S: Sen. G: Chowdhurv. KD: Sadhukhan. GC. (2015). Treatment with garlic

restores membrane thiol content and ameliorates lead induced early death of erythrocytes in mice. Environ
Toxicol 30: 396-410. http ://dx.doi.org/10.1002/tox.21901.

Shah. F: Kazi. TG: Afridi. HI: Baig. JA: Khan. S: Kolachi. NF: Wadhwa. SK: Shah. AO. (2010). Enviromnental

exposure of lead and iron deficit anemia in children age ranged 1-5 years: A cross sectional study. Sci Total
Environ 408: 5325-5330. http://dx.doi.Org/10.1016/i.scitotenv.2010.07.091.

Shanna. V: Shanna. A: Kansal. L. (2010). The effect of oral administration of Allium sativum extracts on lead
nitrate induced toxicity in male mice. Food Chem Toxicol 48: 928-936.
http://dx.doi.Org/10.l6l6/i.fct.2010.01.002.

Shin. JH: Lim. KM: Noh. JY: Bae. ON: Chung. SM: Lee. MY: Chung. JH. (2007). Lead-induced procoagulant

activation of erythrocytes through phosphatidylserine exposure may lead to thrombotic diseases. Chem Res
Toxicol 20: 38-43. http://dx.doi.org/10.1021/tx060114+.

Simons. TJ. (1986). Passive transport and binding of lead by human red blood cells. J Physiol 378: 267-286.
http://dx.doi.org/10.1113/jphvsiol. 1986.sp016219.

Simons. TJB. (1993). Lead transport and binding by human erythrocytes in vitro. Pflugers Arch 423: 307-313.
http://dx.doi.org/10.1007/BF0037441Q.

Simsek. N: Karadeniz. A: Kalkan. Y: Keles. ON: Unal. B. (2009). Spirulina platensis feeding inhibited the anemia-
and leucopenia-induced lead and cadmium in rats. J Hazard Mater 164: 1304-1309.
http://dx.doi.Org/10.1016/i.ihazmat.2008.09.041.

Terayama. K: Maehara. N: Muratsugu. M: Makino. M: Yamamura. K. (1986). Effect of lead on electrophoretic

mobility of rat erythrocytes. Toxicology 40: 259-265. http://dx.doi.org/10.1016/0300-483X(86)90058-2.

U.S. EPA. (2006). Air quality criteria for lead [EPA Report]. (EPA/600/R-05/144aF-bF). Research Triangle Park,
NC. https://cfpub.epa.gov/ncea/risk/recordisplav.cfm?deid=158823.

U.S. EPA. (2013). Integrated science assessment for lead [EPA Report]. (EPA/600/R-10/075F). Washington, DC.
https://nepis.epa.gov/Exe/ZvPURL.cgi?Dockey=P100K82L.txt.

U.S. EPA. (2015). Preamble to the Integrated Science Assessments [EPA Report]. (EPA/600/R-15/067). Research

Triangle Park, NC: U.S. Enviromnental Protection Agency, Office of Research and Development, National

Center for Enviromnental Assessment, RTP Division.

https ://cfpub .epa. gov/ncea/isa/recordisplav. cfm?deid=310244.

Ukaeiiofo. EO: Thomas. N: Ike. SO. (2009). Haematological assessment of occupational exposure to lead handlers
in Enugu urban, Enugu State, Nigeria. Niger J Clin Pract 12: 58-64.

Velaga. MK: Daughtrv. LK: Jones. AC: Yallapragada. PR: Raianna. S: Raianna. B. (2014). Attenuation of lead-
induced oxidative stress in rat brain, liver, kidney and blood of male Wistar rats by Moringa oleifera seed
powder. J Environ Pathol Toxicol Oncol 33: 323-337.
http://dx.doi.org/10.1615/JEnvironPatholToxicolOncol.2014011656.

Wang. O: Zhao. HH: Chen. JW: Hao. OL: Gu. KD: Zhu. YX: Zhou. YK: Ye. LX. (2010a). 5-Aminolevulinic acid
dehydratase activity, urinary 5-aminolevulinic acid concentration and zinc protoporphyrin level among
people with low level of lead exposure. Int J Hyg Environ Health 213: 52-58.
http://dx.doi.Org/10.1016/i.iiheh.2009.08.003.

7-36


-------
Wang. TL: Kao. TH: Inbarai. BS: Su. YT: Chen. BH. (2010b). Inhibition effect of poly(y-glutamic acid) on lead-
induced toxicity in mice. J Agric Food Chem 58: 12562-12567. http://dx.doi.org/10.1021/iflQ34509.

Wang. X: Wang. L: Liu. S. (2015). Heme-regulated eIF2a kinase plays a crucial role in protecting erythroid cells

against Pb-induced hemolytic stress. Chem Res Toxicol 28: 460-469. http://dx.doi.org/10.1021/tx500422q.

Whittaker. MH: Wang. G: Chen. XO: Lipskv. M: Smith. D: Gwiazda. R: Fowler. BA. (2011). Exposure to Pb, Cd,
and As mixtures potentiates the production of oxidative stress precursors: 30-day, 90-day, and 180-day
drinking water studies in rats. Toxicol Appl Pharmacol 254: 154-166.
http://dx.doi.Org/10.1016/i.taap.2010.10.025.

Zou. Y: Feng. W: Wang. W: Chen. Y: Zhou. Z: Li. O: Zhao. T: Mao. G: Wu. X: Yang. L. (2015). Protective effect
of porcine cerebral hydrolysate peptides on learning and memory deficits and oxidative stress in lead-
exposed mice. Biol Trace Elem Res 168: 429-440. http://dx.doi.org/10.1007/sl2011-015-0329-Q.

7-37


-------